Evidence map›Paper›PMID 9077527›Full record

ArticleThe Journal of clinical investigation1997

Pex/PEX tissue distribution and evidence for a deletion in the 3' region of the Pex gene in X-linked hypophosphatemic mice.

L Beck, Y Soumounou, J Martel, G Krishnamurthy, C Gauthier, C G Goodyer, H S Tenenhouse

Open access · bronzeAbstract read
In one paragraph

Article in The Journal of clinical investigation, 1997. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Cited by 71 papers.

0numbers the graph read from it
0cells of the map it votes in
71citing papers in PubMed
14.8field-weighted citation impact, top 1% of its field
1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

Trials whose registry record cites this paper, or whose number appears in the abstract. A trial that started after this paper was published is citing it as background, not reporting it.

Neither the registry nor the abstract names a trial number. If this is a trial report, that itself is worth knowing.

3 · Its place in the literature

Who cites it

71 citing papers in PubMed, 289 citations in OpenAlex.

  1. Article
  2. Review
  3. Article
  4. X-linked hypophosphatemic rickets: from diagnosis to management.Clinical and experimental pediatrics · 2024
    Article
  5. Review
  6. Article
  7. Single-cell RNA sequencing identifiesFrontiers in physiology · 2023
    Article
  8. Article
  9. Review
  10. Molecular Diagnoses of X-Linked and Other Genetic Hypophosphatemias: Results From a Sponsored Genetic Testing Program.Journal of bone and mineral research : the official journal of the American Society for Bone and Mineral Research · 2022
    Article
  11. Review
  12. FGF23 and Hypophosphatemic Rickets/Osteomalacia.Current osteoporosis reports · 2021
    Review
  13. The Causes of Hypo- and Hyperphosphatemia in Humans.Calcified tissue international · 2021
    Review
  14. FGF23 and Associated Disorders of Phosphate Wasting.Pediatric endocrinology reviews : PER · 2019
    Review
  15. Pharmacological management of X-linked hypophosphataemia.British journal of clinical pharmacology · 2019
    Review
  16. Sustained Klotho delivery reduces serum phosphate in a model of diabetic nephropathy.Journal of applied physiology (Bethesda, Md. : 1985) · 2019
    Article
  17. A novelHuman genome variation · 2019
    Article
  18. Review
  19. Article
  20. Review

11 more citing papers are in PubMed but not listed here.

4 · The record

Corrections and comments

PubMed lists nothing against this paper. Absence here is not a guarantee, only a check that was made.

5 · Who and what money

Authors and funding

7 authors at 2 institutions in 1 country.

L BeckDepartment of Pediatrics, McGill University-Montreal Children's Hospital Research Institute, Quebec, Canada.
Y Soumounou
J Martel
G Krishnamurthy
C Gauthier
C G Goodyer
H S Tenenhouse
Montreal Children's Hospital · CAMcGill University · CA

Funding

No grant is acknowledged in the PubMed record.

6 · The paper itself

Abstract

PEX, a phosphate-regulating gene with homology to endopeptidases on the X chromosome, was recently identified as the candidate gene for X-linked hypophosphatemia. In the present study, we cloned mouse and human Pex/PEX cDNAs encoding part of the 5' untranslated region, the protein coding region, and the entire 3' untranslated region, determined the tissue distribution of Pex/PEX mRNA, and characterized the Pex mutation in the murine Hyp homologue of the human disease. Using the reverse transcriptase/polymerase chain reaction (RT/PCR) and ribonuclease protection assays, we found that Pex/PEX mRNA is expressed predominantly in human fetal and adult mouse calvaria and long bone. With RNA from Hyp mouse bone, an RT/PCR product was generated with 5' but not 3' Pex primer pairs and a protected Pex mRNA fragment was detected with 5' but not 3' Pex riboprobes by ribonuclease protection assay. Analysis of the RT/PCR product derived from Hyp bone RNA revealed an aberrant Pex transcript with retention of intron sequence downstream from nucleotide 1302 of the Pex cDNA. Pex mRNA was not detected on Northern blots of poly (A)+ RNA from Hyp bone, while a low-abundance Pex transcript of approximately 7 kb was apparent in normal bone. Southern analysis of genomic DNA from Hyp mice revealed the absence of hybridizing bands with cDNA probes from the 3' region of the Pex cDNA. We conclude that Pex/PEX is a low-abundance transcript that is expressed predominantly in bone of mice and humans and that a large deletion in the 3' region of the Pex gene is present in the murine Hyp homologue of X-linked hypophosphatemia.

Indexed as

Gene DeletionGenetic LinkageX ChromosomeAmino Acid SequenceAnimalsBase SequenceCloning, MolecularDNA, ComplementaryFemaleFetusHumansHypophosphatemiaMaleMiceMice, Inbred C57BLMice, Mutant StrainsDNA, ComplementaryPHEX Phosphate Regulating Neutral EndopeptidasePHEX protein, humanPhex protein, mouseProteinsRNA, Messenger

Identifiers

PMID9077527
PMCPMC507933
OpenAlexW2000736072

What OpenQuestion holds

Textmetadata
Read underepoch 390

Registered trials

None linked

Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the OpenQuestion graph.