Evidence map›Paper›PMID 42872042›Full record

ArticleFrontiers in pediatrics2026

Engaging children, adolescents and young adults living with rare diseases as research partners: practical considerations for meaningful involvement.

Maria Cavaller-Belaubi, Elena-Alexandra Tataru, Donato Bonifazi, Daniel J O'Connor, Francis P Crawley, Michelle A Farrar, Segolene Gaillard, Ainara Gómez Puigvert, Diana Kwast-Hoekstra, Louise Kearney and 4 more

Abstract read
In one paragraph

Article in Frontiers in pediatrics, 2026. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Not yet cited in PubMed.

0numbers the graph read from it
0cells of the map it votes in
0citing papers in PubMed
–field-weighted citation impact
1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

Trials whose registry record cites this paper, or whose number appears in the abstract. A trial that started after this paper was published is citing it as background, not reporting it.

Neither the registry nor the abstract names a trial number. If this is a trial report, that itself is worth knowing.

3 · Its place in the literature

Who cites it

0 citing papers in PubMed.

No citing paper in PubMed yet.

4 · The record

Corrections and comments

PubMed lists nothing against this paper. Absence here is not a guarantee, only a check that was made.

5 · Who and what money

Authors and funding

14 authors.

Maria Cavaller-BelaubiEURORDIS-Rare Diseases Europe, Paris, France.
Elena-Alexandra TataruInternational Rare Diseases Research Consortium (IRDiRC), Paris, France.
Donato BonifaziTEDDY- European Network of Excellence for Paediatric Clinical Research, Bari, Italy.
Daniel J O'ConnorThe Association of the British Pharmaceutical Industry (ABPI), London, United Kingdom.
Francis P CrawleyGood Clinical Practice Alliance (GCPA) Europe, Bruxelles, Belgium.
Michelle A FarrarDepartment of Neurology, Sydney Children's Hospitals Network, Sydney, NSW, Australia.
Segolene GaillardCIC Inserm, Kids France, CHU-Lyon, Lyon, France.
Ainara Gómez PuigvertYPAG Kids Barcelona, Barcelona, Spain.
Diana Kwast-HoekstraInternational Rare Diseases Research Consortium (IRDiRC), Paris, France.
Louise KearneyFortrea, Kingston Upon Thames, United Kingdom.
Samantha ParkerInternational Rare Diseases Research Consortium (IRDiRC), Paris, France.
Sabina Schmidt Goldstein-BecerraThe International Children's Advisory Network, Los Angeles, CA, United States.
Karsten Vanden WynagertGhent University Hospital, Ghent, Belgium.
Anneliene H JonkerInternational Rare Diseases Research Consortium (IRDiRC), Paris, France.

Funding

No grant is acknowledged in the PubMed record.

6 · The paper itself

Abstract

Engagement of patients has become increasingly recognized as an important principle in medical and health research and development. However, the engagement of young people affected by a rare disease- including children, adolescents, and young adults - has lacked consistent practical guidance that is structured, developmentally appropriate, and ethically grounded. Without clearer practical considerations, researchers may have limited guidance to effectively include this crucial population in ways that respect their evolving autonomy, accommodate diverse contexts, and ensure meaningful impact. This is especially important in rare disease research, where the majority of affected people are children. To address this gap, the International Rare Diseases Research Consortium convened a Working Group on Young People's Engagement, comprising 16 international experts. The group included two young people alongside academic and industry researchers, patient advocates, and clinical specialists with experience working directly with youth. The Working Group reviewed core requirements for engaging young people in research and examined case studies illustrating diverse engagement approaches. Drawing on existing patient engagement frameworks, the group developed expert-informed practical guidance, including a checklist, to support researchers in considering appropriate engagement strategies across developmental stages and research contexts. Strengthening the engagement of young people in rare disease research may help ensure that different types of research, including innovation development, shaping study design, outcome measures and policy decisions, are meaningful, relevant, and reflective of their lived experiences.

Indexed as

childrenpatient engagementrare diseasesresearch and developmenttherapy developmentyoung people

Identifiers

PMID42872042
PMCPMC13659889

What OpenQuestion holds

Textmetadata
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Registered trials

None linked

Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the OpenQuestion graph.