Evidence map›Paper›PMID 42568413›Full record

ArticleFrontiers in immunology2026

Data-augmented machine learning refines the effective-concentration estimate for eculizumab in complement-mediated diseases.

Francisco J Fernández, Lucía Alfonso-González, Manuel Praga, Kaare Mikkelsen, M Cristina Vega

Abstract read
In one paragraph

Article in Frontiers in immunology, 2026. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Not yet cited in PubMed.

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1 · What the graph read from it

What it found

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The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

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3 · Its place in the literature

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4 · The record

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5 · Who and what money

Authors and funding

5 authors.

Francisco J Fernández *Dep. Molecular and Cellular Biosciences, Centro de Investigaciones Biológicas Margarita Salas (CIB-CSIC), Consejo Superior de Investigaciones Científicas, Madrid, Spain.
Lucía Alfonso-GonzálezDep. Molecular and Cellular Biosciences, Centro de Investigaciones Biológicas Margarita Salas (CIB-CSIC), Consejo Superior de Investigaciones Científicas, Madrid, Spain.
Manuel PragaDepartment of Medicine, Complutense University, Madrid, Spain.
Kaare MikkelsenDepartment of Electrical and Computer Engineering, Aarhus University, Aarhus, Denmark.
M Cristina Vega *Dep. Molecular and Cellular Biosciences, Centro de Investigaciones Biológicas Margarita Salas (CIB-CSIC), Consejo Superior de Investigaciones Científicas, Madrid, Spain.

Funding

No grant is acknowledged in the PubMed record.

6 · The paper itself

Abstract

Eculizumab, a humanized monoclonal antibody targeting the complement protein C5, is highly efficient in paroxysmal nocturnal hemoglobinuria, atypical hemolytic uremic syndrome, generalized myasthenia gravis, and neuromyelitis optica spectrum disorder. However, recent reports have highlighted a subset of patients who show inadequate treatment response, prompting dose escalation or interval shortening. The serum concentration required for sustained inhibition of the complement lytic pathway remains uncertain, and the commonly cited 50-100 µg/ml range is not grounded in robust pharmacokinetic-pharmacodynamic data. Using publicly available clinical data digitized from four rare indications, we trained machine-learning supervised classifiers to predict complete C5 inhibition as a function of serum eculizumab concentration, identifying logistic regression on log-transformed concentration as the best and mechanistically appropriate model on real data. We then examined whether augmenting the real training data with high-fidelity synthetic data improves the resulting estimate. Although augmentation did not significantly change balanced accuracy, it reduced the confidence interval for the effective concentration by roughly 12-fold (a 92% reduction). The augmentation-stabilized estimate of the concentration associated with complete C5 inhibition was approximately 310.8-335.2 µg/ml (real-data-only estimate 338 µg/ml, 95% CI 275-454). These data-driven, hypothesis-generating results indicate that current maintenance targets aimed at near-complete C5 suppression may be substantially underestimated and that faithful synthetic augmentation can improve the precision of model-based pharmacological estimates in rare diseases; prospective validation in independent cohorts is required before any clinical application.

Indexed as

Antibodies, Monoclonal, HumanizedComplement C5Complement Inactivating AgentsMachine LearningAtypical Hemolytic Uremic SyndromeHemoglobinuria, ParoxysmalHumansMyasthenia GravisNeuromyelitis OpticaTreatment OutcomeAntibodies, Monoclonal, HumanizedComplement C5Complement Inactivating Agentseculizumabatypical hemolytic uremic syndrome (aHUS)complement factor C5complement systemeculizumab (monoclonal antibody to C5)machine learning (ML)paroxysmal nocturnal hemoglobinuria (PNH)synthetic data augmentation

Identifiers

PMID42568413
PMCPMC13447158

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Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the OpenQuestion graph.