Evidence map›Paper›PMID 42483184›Full record

ReviewFrontiers in immunology2026

Individualized repetitive intravenous immunoglobulin therapy for a 79-year-old patient with GlyR antibody-positive PERM: a case report and literature review.

Xiaojun Liu, Jianwei Zhu, Yuanhong Lei, Xinyuan Yu, Xiujuan Mi

Abstract readCase ReportsReview
In one paragraph

Review in Frontiers in immunology, 2026. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Not yet cited in PubMed.

0numbers the graph read from it
0cells of the map it votes in
0citing papers in PubMed
–field-weighted citation impact
1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

Trials whose registry record cites this paper, or whose number appears in the abstract. A trial that started after this paper was published is citing it as background, not reporting it.

Neither the registry nor the abstract names a trial number. If this is a trial report, that itself is worth knowing.

3 · Its place in the literature

Who cites it

0 citing papers in PubMed.

No citing paper in PubMed yet.

4 · The record

Corrections and comments

PubMed lists nothing against this paper. Absence here is not a guarantee, only a check that was made.

5 · Who and what money

Authors and funding

5 authors.

Xiaojun Liu *Department of Encephalopathy, Chongqing Traditional Chinese Medicine Hospital (The First Affiliated Hospital of Chongqing University of Chinese Medicine), Chongqing, China.
Jianwei Zhu *Department of Encephalopathy, Chongqing Traditional Chinese Medicine Hospital (The First Affiliated Hospital of Chongqing University of Chinese Medicine), Chongqing, China.
Yuanhong LeiDepartment of Encephalopathy, Chongqing Traditional Chinese Medicine Hospital (The First Affiliated Hospital of Chongqing University of Chinese Medicine), Chongqing, China.
Xinyuan YuDepartment of Encephalopathy, Chongqing Traditional Chinese Medicine Hospital (The First Affiliated Hospital of Chongqing University of Chinese Medicine), Chongqing, China.
Xiujuan MiDepartment of Encephalopathy, Chongqing Traditional Chinese Medicine Hospital (The First Affiliated Hospital of Chongqing University of Chinese Medicine), Chongqing, China.

Funding

No grant is acknowledged in the PubMed record.

6 · The paper itself

Abstract

Progressive encephalomyelitis with rigidity and myoclonus (PERM) is a rare, life-threatening variant of stiff-person spectrum disorder that is primarily associated with anti-glycine receptor (GlyR) antibodies. Although advanced age and intensive care unit admission have been associated with poor outcomes for patients with GlyR antibody-positive PERM, detailed management strategies for elderly patients with multiple comorbidities remain limited. We report the successful individualized management of a 79-year-old male with glycine receptor 1 (GlyR1) antibody-positive PERM, who is among the oldest reported survivors of severe PERM. The patient initially presented with paroxysmal limb spasms, which were misattributed to spinal degeneration and a minor thalamic infarction. The subsequent development of a prominent startle response, respiratory failure, and autonomic instability prompted an autoimmune evaluation, confirming the presence of anti-GlyR1 antibodies in both serum and cerebrospinal fluid. High-dose corticosteroid pulse therapy was avoided because of an active pulmonary infection and comorbidity-related safety concerns. Intravenous immunoglobulin (IVIg) was selected as the initial immunomodulatory therapy, while plasma exchange was deferred and later discontinued after a single session because of procedure-related complications and hemodynamic instability. The patient received three sequential courses of IVIg; in addition, a single 20-mg subcutaneous dose of ofatumumab was administered as individualized off-label sequential/salvage immunotherapy. A major clinical improvement, including a reduction in spasms, successful extubation, antibody seroconversion, and excellent functional recovery with a modified Rankin scale (mRS) score of 1, occurred after repeated IVIg courses. At the 12-month follow-up, the patient remained clinically stable and had sustained negative GlyR1 antibody results. This case report highlights the importance of the early recognition of stimulus-sensitive spasms and the startle response in elderly patients with misleading age-related imaging findings. These findings also suggest that repeated IVIg courses may represent a feasible salvage strategy when conventional immunotherapies are limited, but the independent therapeutic contribution of ofatumumab remains uncertain. Serial GlyR1 antibody titers may be useful for monitoring the treatment response, although this result requires confirmation in larger studies.

Indexed as

AutoantibodiesEncephalomyelitisImmunoglobulins, IntravenousMuscle RigidityMyoclonusReceptors, GlycineStiff-Person SyndromeAgedHumansMaleTreatment OutcomeAutoantibodiesImmunoglobulins, IntravenousReceptors, Glycinecase reportglycine receptor antibodyintravenous immunoglobulinprogressive encephalomyelitis with rigidity and myoclonusstiff-person syndrome

Identifiers

PMID42483184
PMCPMC13385179

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Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the OpenQuestion graph.