Evidence map›Paper›PMID 41804000›Full record

ArticleJournal of medical case reports2026

Localized cystic dilatation of the intrahepatic bile ducts as a distinct subtype of Caroli disease: a case report.

Shoko Kato, Kenitiro Kaneko, Takuo Noda, Hiroshi Nouso, Yasuyuki Fukami, Tsuyoshi Sano

Abstract readCase Reports
PubMed Full text at PMC Publisher
In one paragraph

Article in Journal of medical case reports, 2026. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Not yet cited in PubMed.

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1 · What the graph read from it

What it found

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The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

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3 · Its place in the literature

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4 · The record

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5 · Who and what money

Authors and funding

6 authors.

Shoko KatoDepartment of Gastroenterological Surgery, Aichi Medical University, 1-1 Yazakokarimata, Nagakute, Aichi, 480-1195, Japan. shokodayo56@yahoo.co.jp.ORCID http://orcid.org/0000-0003-4645-5556
Kenitiro KanekoDepartment of Gastroenterological Surgery, Aichi Medical University, 1-1 Yazakokarimata, Nagakute, Aichi, 480-1195, Japan.
Takuo NodaDepartment of Pediatric Surgery, Okayama University, Kita-Ku, Okayama, Japan.
Hiroshi NousoDepartment of Pediatric Surgery, Okayama University, Kita-Ku, Okayama, Japan.
Yasuyuki FukamiDepartment of Gastroenterological Surgery, Aichi Medical University, 1-1 Yazakokarimata, Nagakute, Aichi, 480-1195, Japan.
Tsuyoshi SanoDepartment of Gastroenterological Surgery, Aichi Medical University, 1-1 Yazakokarimata, Nagakute, Aichi, 480-1195, Japan.

Funding

No grant is acknowledged in the PubMed record.

6 · The paper itself

Abstract

backgroundCaroli disease encompasses multiple distinct entities. We report two cases of localized cystic dilatation of the intrahepatic bile ducts exhibiting a unique morphology. CASE PRESENTATIONS: Both patients were Japanese, diagnosed with a cyst in the liver prenatally (27 weeks' gestation) and at 3 months of age. The dilatation was limited to the anterior section branch and its first upstream branches, and the cystically dilated bile ducts abruptly connected to normal-sized ducts on both the upstream and downstream sides. One case transiently had debris in the dilated duct during the neonatal period, but did not present any symptoms. The patients have remained asymptomatic for 10 years (case 1) and 9 years (case 2).

conclusionThis case report presents a distinct entity separate from other forms of Caroli disease, namely, localized cystic dilatation of the intrahepatic bile ducts. In total, 12 cases, along with 10 similar cases from literature, were assessed.

Indexed as

Bile Ducts, IntrahepaticCaroli DiseaseCystsChildDilatation, PathologicFemaleHumansInfantInfant, NewbornMaleCaroli diseaseSolitary intrahepatic biliary cystTodani type V

Identifiers

PMID41804000
PMCPMC13085339

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