Evidence map›Paper›PMID 41751879›Full record

ArticleInternational journal of molecular sciences2026

Sleep-Disordered Breathing in Chung-Jansen Syndrome.

Katerina Vlami, Konstantina Kosma, Lamprini Athanasopoulou, Eirini Kokiou, Vasileios Paraschou, Maria Gerogianni, Stylianos Loukides, Melpomeni Peppa

Abstract readCase Reports
In one paragraph

Article in International journal of molecular sciences, 2026. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Not yet cited in PubMed.

0numbers the graph read from it
0cells of the map it votes in
0citing papers in PubMed
–field-weighted citation impact
1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

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Neither the registry nor the abstract names a trial number. If this is a trial report, that itself is worth knowing.

3 · Its place in the literature

Who cites it

0 citing papers in PubMed.

No citing paper in PubMed yet.

4 · The record

Corrections and comments

PubMed lists nothing against this paper. Absence here is not a guarantee, only a check that was made.

5 · Who and what money

Authors and funding

8 authors.

Katerina Vlami2nd Pulmonary Medicine Department, Medical School, General University Hospital "Attikon", National and Kapodistrian University of Athens, Rimini 1 Str., 12462 Haidari, Greece.
Konstantina KosmaLaboratory of Medical Genetics, St. Sophia's Children's Hospital, National and Kapodistrian University of Athens, 11527 Athens, Greece.ORCID 0000-0002-5826-0556
Lamprini Athanasopoulou2nd Pulmonary Medicine Department, Medical School, General University Hospital "Attikon", National and Kapodistrian University of Athens, Rimini 1 Str., 12462 Haidari, Greece.ORCID 0009-0009-2733-8611
Eirini Kokiou2nd Pulmonary Medicine Department, Medical School, General University Hospital "Attikon", National and Kapodistrian University of Athens, Rimini 1 Str., 12462 Haidari, Greece.
Vasileios Paraschou2nd Pulmonary Medicine Department, Medical School, General University Hospital "Attikon", National and Kapodistrian University of Athens, Rimini 1 Str., 12462 Haidari, Greece.ORCID 0000-0001-6916-2268
Maria GerogianniEndocrine Unit, 2nd Department of Propaedeutic Internal Medicine, Attikon University Hospital, School of Medicine, National and Kapodistrian University of Athens, Rimini 1 Str., 12462 Haidari, Greece.
Stylianos Loukides2nd Pulmonary Medicine Department, Medical School, General University Hospital "Attikon", National and Kapodistrian University of Athens, Rimini 1 Str., 12462 Haidari, Greece.ORCID 0000-0002-4278-9922
Melpomeni PeppaEndocrine Unit, 2nd Department of Propaedeutic Internal Medicine, Attikon University Hospital, School of Medicine, National and Kapodistrian University of Athens, Rimini 1 Str., 12462 Haidari, Greece.ORCID 0000-0002-3538-2534

Funding

No grant is acknowledged in the PubMed record.

6 · The paper itself

Abstract

We report a thirty-six-year-old woman with intellectual disability who was referred for evaluation of suspected obstructive sleep apnea. The initial clinical impression suggested a syndromic case, so comprehensive genetic testing was undertaken. Overnight polysomnography revealed a severe rapid eye movement-predominant obstructive sleep apnea syndrome with an apnea-hypopnea index of 31.9 events per hour, rapid eye movement apnea-hypopnea index of 113.8 events per hour, and lowest oxygen saturation of 66%. Treatment with continuous positive airway pressure improved respiratory and sleep quality indices and was well tolerated. Whole-exome sequencing identified a de novo splice site variant in the pleckstrin homology domain interacting protein gene (c.41-1G > A), confirming a molecular diagnosis of Chung-Jansen Syndrome. Chung-Jansen syndrome is a rare neurodevelopmental disorder caused by heterozygous pathogenic variants in the pleckstrin homology domain interacting protein gene, marked by developmental delay, intellectual disability, behavioral abnormalities, dysmorphism, and progressive obesity. PHIP influences central and peripheral pathways controlling satiety, pancreatic function, and body weight. Despite frequent reports of sleep problems, systematic evaluation of sleep-disordered breathing has been limited. This adult case provides the first polysomnographic confirmation in the syndrome, supporting proactive screening for obstructive sleep apnea-especially in those with obesity. Integrating genetic assessment into sleep care can reduce diagnostic delays and better guide therapy and prognosis.

Indexed as

Intellectual DisabilitySleep Apnea, ObstructiveSleep Apnea SyndromesAdultFemaleHumansPolysomnographygenetic obesityobstructive sleep apneapleckstrin homology domain interacting protein

Identifiers

PMID41751879
PMCPMC12940234

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Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the OpenQuestion graph.