Evidence map›Paper›PMID 41549917›Full record

ReviewIUBMB life2026

Balancing Promise and Peril: Hemophilia Gene Therapy Insights.

Saicharan Akula, Ester Borroni, Alessia Cottonaro, Antonia Follenzi, Simone Merlin

Abstract readReview
In one paragraph

Review in IUBMB life, 2026. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Cited by 1 paper.

0numbers the graph read from it
0cells of the map it votes in
1citing papers in PubMed
–field-weighted citation impact
1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

Trials whose registry record cites this paper, or whose number appears in the abstract. A trial that started after this paper was published is citing it as background, not reporting it.

Neither the registry nor the abstract names a trial number. If this is a trial report, that itself is worth knowing.

3 · Its place in the literature

Who cites it

1 citing paper in PubMed.

  1. Review
4 · The record

Corrections and comments

PubMed lists nothing against this paper. Absence here is not a guarantee, only a check that was made.

5 · Who and what money

Authors and funding

5 authors.

Saicharan AkulaDepartment of Health Sciences, Università degli Studi del Piemonte Orientale, Novara, Italy.
Ester BorroniDepartment of Health Sciences, Università degli Studi del Piemonte Orientale, Novara, Italy.ORCID 0000-0003-1238-1720
Alessia CottonaroDepartment of Health Sciences, Università degli Studi del Piemonte Orientale, Novara, Italy.
Antonia FollenziDepartment of Health Sciences, Università degli Studi del Piemonte Orientale, Novara, Italy.ORCID 0000-0001-9780-300X
Simone MerlinDepartment of Health Sciences, Università degli Studi del Piemonte Orientale, Novara, Italy.ORCID 0000-0001-5209-3921

Funding

CSP-Compagnia San Paolo Trapezio 68155PNRR MUR-M4C2-CN RNA & GENE THERAPY-Spoke 1
6 · The paper itself

Abstract

Hemophilia is an inherited disorder characterized by impaired blood clotting caused by mutations in the genes responsible for producing coagulation factor (F) VIII (hemophilia A, HA) or FIX (hemophilia B, HB). Current treatment primarily relies on replacement therapy, involving frequent and costly infusions of FVIII or FIX concentrates. While effective, these treatments come with the risk of developing neutralizing antibodies (inhibitors) against the infused factor. In recent years, non-factor replacement therapies have emerged as innovative treatment options, offering enhanced efficacy especially for patients with inhibitors. Despite their advantages, these approaches still fall short of providing a definitive, long-term cure. Since hemophilia is a monogenic disease, it presents an excellent opportunity for cell and gene therapy approaches aimed at achieving durable treatment and potentially a cure. Over the past three decades, remarkable advancements have been made in hemophilia gene therapy, culminating in the approval of Valoctocogene roxaparvovec (ROCTAVIAN, AAV-FVIII) and Etranacogene dezaparvovec (HEMGENIX, AAV-FIX) for patients with severe HA and HB, respectively. Nevertheless, gene therapy poses questions regarding its long-term efficacy and safety. This review synthesizes findings from clinical trials, addresses persistent challenges in hemophilia gene therapy, and underscores the biological constraints and limitations inherent to viral vector-based approaches.

Indexed as

Factor IXFactor VIIIGenetic TherapyHemophilia AHemophilia BAnimalsDependovirusGene Therapy AgentsGenetic VectorsHumansFactor IXFactor VIII

Identifiers

PMID41549917
PMCPMC12813738

What OpenQuestion holds

Textmetadata
LicenceCC BY
Read underepoch 390

Registered trials

None linked

Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the OpenQuestion graph.