Evidence map›Paper›PMID 41495530›Full record

ArticleCEN case reports2026

Congenital nephrotic syndrome in a newborn with glycogen storage disease and Wilms tumor 1 (WT1) mutation.

Luigi Annicchiarico Petruzzelli, Oriana De Marco, Nicola Improda, Paolo Giannattasio, Ilaria Luongo, Martina Carucci, Barbara Brunetti, Vittorio Serio, Bruno Minale, Gabriele Malgieri

Abstract readCase Reports
In one paragraph

Article in CEN case reports, 2026. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Not yet cited in PubMed.

0numbers the graph read from it
0cells of the map it votes in
0citing papers in PubMed
–field-weighted citation impact
1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

Trials whose registry record cites this paper, or whose number appears in the abstract. A trial that started after this paper was published is citing it as background, not reporting it.

Neither the registry nor the abstract names a trial number. If this is a trial report, that itself is worth knowing.

3 · Its place in the literature

Who cites it

0 citing papers in PubMed.

No citing paper in PubMed yet.

4 · The record

Corrections and comments

PubMed lists nothing against this paper. Absence here is not a guarantee, only a check that was made.

5 · Who and what money

Authors and funding

10 authors.

Luigi Annicchiarico Petruzzelli *Pediatric Nephrology, Dialysis and Renal Transplantation, Santobono Pausilipon Children's Hospital, Naples, Italy.
Oriana De Marco *Pediatric Nephrology, Dialysis and Renal Transplantation, Santobono Pausilipon Children's Hospital, Naples, Italy. odemarco1@gmail.com.ORCID 0000-0002-8299-7160
Nicola ImprodaNeuro-endocrine Diseases and Obesity Unit, Department of Neurosciences, Santobono- Pausilipon Children's Hospital, Naples, Italy.
Paolo GiannattasioPediatric Nephrology, Dialysis and Renal Transplantation, Santobono Pausilipon Children's Hospital, Naples, Italy.
Ilaria LuongoPediatric Nephrology, Dialysis and Renal Transplantation, Santobono Pausilipon Children's Hospital, Naples, Italy.
Martina CarucciPediatric Nephrology, Dialysis and Renal Transplantation, Santobono Pausilipon Children's Hospital, Naples, Italy.
Barbara BrunettiPediatric Nephrology, Dialysis and Renal Transplantation, Santobono Pausilipon Children's Hospital, Naples, Italy.
Vittorio SerioPediatric Nephrology, Dialysis and Renal Transplantation, Santobono Pausilipon Children's Hospital, Naples, Italy.
Bruno MinalePediatric Nephrology, Dialysis and Renal Transplantation, Santobono Pausilipon Children's Hospital, Naples, Italy.
Gabriele MalgieriPediatric Nephrology, Dialysis and Renal Transplantation, Santobono Pausilipon Children's Hospital, Naples, Italy.

Funding

No grant is acknowledged in the PubMed record.

6 · The paper itself

Abstract

Genetic disorders in neonates often present with overlapping clinical features, posing significant diagnostic challenges. Glycogen storage diseases (GSD) disrupt glycogen metabolism, leading to energy deficits. Pathogenic variants in the Wilms tumor 1 (WT1) gene represent a rare but significant cause of early-onset steroid-resistant nephrotic syndrome (SRNS), associated with a broad range of both kidney and extrakidney phenotypic manifestations. The coexistence of these genetic diseases in a single patient has not been previously reported. Herein, we present a case of a newborn with symptomatic hypoglycemia and metabolic acidosis that was transferred to the Neonatal Intensive Care Unit. During hospitalization, he developed hyponatremia and nephrotic-range proteinuria, a genetic test was performed, and he was transferred to the nephrology unit. Genetic analysis identified a compound homozygous mutation (c.247 C > T) in the G6PC gene, confirming glycogen storage disease type 1a (GSD-1a) and a pathogenic WT1 mutation (c.1400G > A) associated with Denys-Drash syndrome. This case highlights the importance of a multidisciplinary approach in the evaluation and management of neonates with a complex combination of genetically-determined conditions.

Indexed as

Denys-Drash SyndromeGlycogen Storage DiseaseGlycogen Storage Disease Type INephrotic SyndromeWT1 ProteinsGlucose-6-PhosphataseHumansInfant, NewbornMaleMutationGlucose-6-PhosphataseWT1 protein, humanWT1 ProteinsGenetic diseaseGlycogen storage diseasesNephrotic syndromeWT1 mutation

Identifiers

PMID41495530
PMCPMC12775229

What OpenQuestion holds

Textmetadata
Read underepoch 390

Registered trials

None linked

Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the OpenQuestion graph.