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ArticleInternational medical case reports journal2025

Homozygous α-Spectrin (SPTA1) Variant Causing Persistent Hereditary Pyropoikilocytosis in a Newborn: A Case Report and Literature Review.

Jamal Sayed, Alanoud Sulaiman Alabdulhadi, Waheed Abdullah Alzahrani, Faisal Joueidi, Ghaida Ali Alzahrani, Ahmed Gamal Sayed, Gamal T Ebid

Abstract readCase Reports
In one paragraph

Article in International medical case reports journal, 2025. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Not yet cited in PubMed.

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4 · The record

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5 · Who and what money

Authors and funding

7 authors.

Jamal SayedDepartment of Pediatrics, Security Forces Hospital Makkah, (SFHM), Makkah, Saudi Arabia.ORCID 0000-0002-2087-9601
Alanoud Sulaiman AlabdulhadiCollege of Medicine, Alfaisal University, Riyadh, 11533, Saudi Arabia.ORCID 0009-0001-9459-764X
Waheed Abdullah AlzahraniDepartment of Pediatrics, Security Forces Hospital Makkah, (SFHM), Makkah, Saudi Arabia.
Faisal JoueidiCollege of Medicine, Alfaisal University, Riyadh, 11533, Saudi Arabia.ORCID 0009-0002-5570-4120
Ghaida Ali AlzahraniIbn Sina National College for Medical Studies, Jeddah, Saudi Arabia.ORCID 0009-0006-8864-889X
Ahmed Gamal SayedCollege of Medicine, Alfaisal University, Riyadh, 11533, Saudi Arabia.
Gamal T EbidDepartment of Pediatrics, Security Forces Hospital Makkah, (SFHM), Makkah, Saudi Arabia.ORCID 0000-0003-0629-1884

Funding

No grant is acknowledged in the PubMed record.

6 · The paper itself

Abstract

Hereditary pyropoikilocytosis is an inherited, rare form of severe hemolytic anemia that is associated with a disordered erythrocyte membrane. Such a disordered membrane is due to the quantitative and qualitative α-spectrin defects that associate with homozygous or doubly heterozygous mutations in the SPTA1 gene. Characterized by marked poikilocytosis, anisocytosis, and thermal sensitivity of erythrocytes, often leading to severe hemolytic anemia and neonatal jaundice. We report the case of a full-term newborn admitted in the first day of life to the neonatal intensive care unit with significant jaundice and anemia. Peripheral blood smear revealed severe anemia with pronounced anisopoikilocytosis and moderate elliptocytosis, suggestive of a hereditary RBC membrane disorder. The whole exome sequencing (WES) did identify a SPTA1 gene homozygous likely pathogenic missense variant, p. (Leu260Pro) confirming the diagnosis of hereditary pyropoikilocytosis. The patient received intensive phototherapy and a red blood cell transfusion during hospitalization. Over an 18-month follow-up period, the infant remained clinically stable with no further transfusion requirements. However, the features consistent with HPP tended to be persistent during the follow‑up, highlighting the chronic nature of the disorder in this case. Furthermore, it underscores the importance of considering rare hereditary causes of hemolytic anemia in neonates presenting with early-onset jaundice and anemia. It highlights the diagnostic value of genetic testing in confirming SPTA1-related disorders.

Indexed as

hereditary anemianeonatal pyropoikilocytosisneonatal red cell membrane disorder

Identifiers

PMID41098499
PMCPMC12520006

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