Evidence map›Paper›PMID 40869958›Full record

ArticleGenes2025

Clinical and Genetic Management of a Patient with Rubinstein-Taybi Syndrome Type 1: A Case Report.

Victor Santos, Pedro Paulo Chaves de Souza, Talyta Campos, Hiane Winterly, Thaís Vieira, Marc Gigonzac, Alex Honda, Irene Pinto, Raffael Zatarin, Fernando Azevedo and 3 more

Abstract readCase Reports
In one paragraph

Article in Genes, 2025. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Not yet cited in PubMed.

0numbers the graph read from it
0cells of the map it votes in
0citing papers in PubMed
–field-weighted citation impact
1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

Trials whose registry record cites this paper, or whose number appears in the abstract. A trial that started after this paper was published is citing it as background, not reporting it.

Neither the registry nor the abstract names a trial number. If this is a trial report, that itself is worth knowing.

3 · Its place in the literature

Who cites it

0 citing papers in PubMed.

No citing paper in PubMed yet.

4 · The record

Corrections and comments

PubMed lists nothing against this paper. Absence here is not a guarantee, only a check that was made.

5 · Who and what money

Authors and funding

13 authors.

Victor SantosGraduate Program in Genetics and Molecular Biology, Federal University of Goiás, Goiânia 74605-050, GO, Brazil.ORCID 0009-0007-8155-8098
Pedro Paulo Chaves de SouzaGraduate Program in Genetics and Molecular Biology, Federal University of Goiás, Goiânia 74605-050, GO, Brazil.ORCID 0000-0001-7266-6061
Talyta CamposGraduate Program in Genetics and Molecular Biology, Federal University of Goiás, Goiânia 74605-050, GO, Brazil.ORCID 0009-0000-0540-570X
Hiane WinterlyReplicon Research Nucleus, Graduate Program in Genetics, School of Medical and Life Sciences, Pontifical Catholic University of Goiás, Goiânia 74605-050, GO, Brazil.ORCID 0009-0009-2404-444X
Thaís VieiraReplicon Research Nucleus, Graduate Program in Genetics, School of Medical and Life Sciences, Pontifical Catholic University of Goiás, Goiânia 74605-050, GO, Brazil.ORCID 0000-0002-2111-132X
Marc GigonzacReplicon Research Nucleus, Graduate Program in Genetics, School of Medical and Life Sciences, Pontifical Catholic University of Goiás, Goiânia 74605-050, GO, Brazil.
Alex HondaReplicon Research Nucleus, Graduate Program in Genetics, School of Medical and Life Sciences, Pontifical Catholic University of Goiás, Goiânia 74605-050, GO, Brazil.
Irene PintoGraduate Program in Genetics and Molecular Biology, Federal University of Goiás, Goiânia 74605-050, GO, Brazil.
Raffael ZatarinClinical Genetics Service, Center for Rehabilitation and Readaptation Dr. Henrique Santillo, State Health Department of Goiás, Goiânia 74605-050, GO, Brazil.
Fernando AzevedoGraduate Program in Genetics and Molecular Biology, Federal University of Goiás, Goiânia 74605-050, GO, Brazil.ORCID 0000-0002-8623-374X
Anna NascimentoClinical Genetics Service, Center for Rehabilitation and Readaptation Dr. Henrique Santillo, State Health Department of Goiás, Goiânia 74605-050, GO, Brazil.
Cláudio da SilvaReplicon Research Nucleus, Graduate Program in Genetics, School of Medical and Life Sciences, Pontifical Catholic University of Goiás, Goiânia 74605-050, GO, Brazil.
Aparecido da CruzGraduate Program in Genetics and Molecular Biology, Federal University of Goiás, Goiânia 74605-050, GO, Brazil.ORCID 0000-0003-0753-3814

Funding

No grant is acknowledged in the PubMed record.

6 · The paper itself

Abstract

Rubinstein-Taybi Syndrome type 1 (RSTS1) is an uncommon autosomal dominant genetic disorder associated with neurodevelopmental impairments and multiple congenital anomalies, with an incidence of 1:100,000-125,000 live births. The syndrome, caused by de novo mutations in the CREBBP gene, is characterized by phenotypic variability, including intellectual disability, facial dysmorphisms, and systemic abnormalities. The current case report describes a 15-year-old Brazilian female diagnosed with RSTS1 through whole-exome sequencing, which identified a de novo heterozygous missense mutation in the CREBBP gene (NM_004380.3; c.4393G > C; p.Gly1465Arg), classified as pathogenic. The patient's clinical presentation included facial dysmorphisms, skeletal abnormalities, neurodevelopmental delay, psychiatric conditions, and other systemic manifestations. A comprehensive genetic counseling process facilitated the differential diagnosis and management strategies, emphasizing the importance of early and precise diagnosis for improving clinical outcomes. This report contributes to the growing knowledge of the genotype-phenotype correlations in RSTS1, aiding in the understanding and management of this uncommon condition.

Indexed as

CREB-Binding ProteinRubinstein-Taybi SyndromeAdolescentExome SequencingFemaleGenetic Association StudiesHumansMutation, MissensePhenotypeCREB-Binding ProteinCREBBP protein, humanbroad thumbsCREBBPfacial dysmorphismsGDDIDuncommon disease

Identifiers

PMID40869958
PMCPMC12385857

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Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the OpenQuestion graph.