Evidence map›Paper›PMID 40808971›Full record

ArticleIEEE access : practical innovations, open solutions2025

A 3D Clinical Face Phenotype Space of Genetic Syndromes Using a Triplet-Based Singular Geometric Autoencoder.

Soha S Mahdi, Eduarda Caldeira, Harold Matthews, Michiel Vanneste, Nele Nauwelaers, Meng Yuan, Giorgos Bouritsas, Gareth S Baynam, Peter Hammond, Richard Spritz and 5 more

Abstract read
In one paragraph

Article in IEEE access : practical innovations, open solutions, 2025. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Cited by 3 papers.

0numbers the graph read from it
0cells of the map it votes in
3citing papers in PubMed
–field-weighted citation impact
1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

Trials whose registry record cites this paper, or whose number appears in the abstract. A trial that started after this paper was published is citing it as background, not reporting it.

Neither the registry nor the abstract names a trial number. If this is a trial report, that itself is worth knowing.

3 · Its place in the literature

Who cites it

3 citing papers in PubMed.

  1. Article
  2. Article
  3. Article
4 · The record

Corrections and comments

PubMed lists nothing against this paper. Absence here is not a guarantee, only a check that was made.

5 · Who and what money

Authors and funding

15 authors.

Soha S MahdiETRO, Vrije Universiteit Brussel, 1050 Ixelles, Belgium.
Eduarda CaldeiraESAT/PSI-UZ Leuven, MIRC, KU Leuven, 3000 Leuven, Belgium.ORCID 0009-0002-4891-0057
Harold MatthewsESAT/PSI-UZ Leuven, MIRC, KU Leuven, 3000 Leuven, Belgium.
Michiel VannesteDepartment of Human Genetics, KU Leuven, 3000 Leuven, Belgium.ORCID 0000-0003-0222-5740
Nele NauwelaersESAT/PSI-UZ Leuven, MIRC, KU Leuven, 3000 Leuven, Belgium.ORCID 0000-0002-9763-6106
Meng YuanESAT/PSI-UZ Leuven, MIRC, KU Leuven, 3000 Leuven, Belgium.ORCID 0000-0003-0922-8012
Giorgos BouritsasArchimedes AI Unit/Athena RC, Department of Informatics and Telecommunications, University of Athens, 115 28 Athens, Greece.ORCID 0000-0002-8476-4918
Gareth S BaynamSchool of Earth and Planetary Sciences, Faculty of Science and Engineering, Curtin University, Perth, WA 6102, Australia.
Peter HammondDepartment of Human Genetics, KU Leuven, 3000 Leuven, Belgium.ORCID 0000-0003-3208-4459
Richard SpritzSchool of Medicine, Human Medical Genetics and Genomics Program, University of Colorado, Aurora, CO 80918, USA.ORCID 0000-0002-8325-0026
Ophir D KleinDepartment of Orofacial Sciences, Institute for Human Genetics, University of California at San Francisco, San Francisco, CA 94143, USA.
Michael BronsteinDepartment of Computer Science, University of Oxford, AX1 3QD Oxford, U.K.
Benedikt HallgrimssonCumming School of Medicine, Department of Cell Biology and Anatomy, University of Calgary, Calgary, AB T2N 1N4, Canada.ORCID 0000-0002-7192-9103
Hilde PeetersDepartment of Human Genetics, KU Leuven, 3000 Leuven, Belgium.
Peter ClaesESAT/PSI-UZ Leuven, MIRC, KU Leuven, 3000 Leuven, Belgium.ORCID 0000-0001-9489-9819

Funding

The Genetic Architecture of Human Facial MorphologyR01DE027023 · NIDCR · UNIVERSITY OF PITTSBURGH AT PITTSBURGH · PI CLAES, PETER, SHAFFER, JOHN R · 2017 to 2024
$5.2M
NIDCR NIH HHS R01 DE027023
6 · The paper itself

Abstract

Clinical diagnosis of syndromes benefits strongly from objective facial phenotyping. This study introduces a novel approach to enhance clinical diagnosis through the development and exploration of a low-dimensional metric space referred to as the clinical face phenotypic space (CFPS). As a facial matching tool for clinical genetics, such CFPS can enhance clinical diagnosis. It helps to interpret facial dysmorphisms of a subject by placing them within the space of known dysmorphisms. In this paper, a triplet loss-based autoencoder developed by geometric deep learning (GDL) is trained using multi-task learning, which combines supervised and unsupervised learning approaches. Experiments are designed to illustrate the following properties of CFPSs that can aid clinicians in narrowing down their search space: a CFPS can 1) classify syndromes accurately, 2) generalize to novel syndromes, and 3) preserve the relatedness of genetic diseases, meaning that clusters of phenotypically similar disorders reflect functional relationships between genes. The proposed model consists of three main components: an encoder based on GDL optimizing distances between groups of individuals in the CFPS, a decoder enhancing classification by reconstructing faces, and a singular value decomposition layer maintaining orthogonality and optimal variance distribution across dimensions. This allows for the selection of an optimal number of CFPS dimensions as well as improving the classification capacity of the CFPS, which outperforms the linear metric learning baseline in both syndrome classification and generalization to novel syndromes. We further proved the usefulness of each component of the proposed framework, highlighting their individual impact. From a clinical perspective, the unique combination of these properties in a single CFPS results in a powerful tool that can be incorporated into current clinical practices to assess facial dysmorphism.

Indexed as

3D shape analysisclinical geneticscomputer-aided diagnosisdeep phenotypinggeometric deep learningprecision public health

Identifiers

PMID40808971
PMCPMC12346114

What OpenQuestion holds

Textmetadata
LicenceCC BY-NC-ND
Read underepoch 390

Registered trials

None linked

Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the OpenQuestion graph.