Evidence map›Paper›PMID 40285338›Full record

ArticleThe American journal of case reports2025

Diagnostic and Therapeutic Challenges in an Acute Variegate Porphyric Crisis Complicated by Anuric Renal Failure and Multiorgan Dysfunction: A Case Report.

Peter B Conroy, Sue Davel, Jacques A J Malherbe, Simon J Carrivick, Edward N Briggs

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Article in The American journal of case reports, 2025. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Not yet cited in PubMed.

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4 · The record

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5 · Who and what money

Authors and funding

5 authors.

Peter B ConroyDepartment of Intensive Care, Joondalup Health Campus, Joondalup, Western Australia, Australia.
Sue DavelDepartment of General Medicine, Joondalup Health Campus, Joondalup, Western Australia, Australia.
Jacques A J MalherbeDepartment of Haematology, Fiona Stanley Hospital, Murdoch, Western Australia, Australia.ORCID 0000-0003-3741-5835
Simon J CarrivickDepartment of Clinical Biochemistry, Pharmacology and Toxicology, PathWest Laboratory Medicine, Nedlands, Western Australia, Australia.
Edward N BriggsDepartment of Intensive Care, Joondalup Health Campus, Joondalup, Western Australia, Australia.

Funding

No grant is acknowledged in the PubMed record.

6 · The paper itself

Abstract

BACKGROUND Acute porphyrias arise from genetic defects in heme synthesis. Significant increases in urine porphobilinogen (PBG) levels are diagnostic, enabling further testing and the commencement of targeted therapies. We report a rare case of an elderly woman with a delayed diagnosis of acute variegate porphyria (VP) neurovisceral crisis, anuria, and multiorgan failure precipitated by methicillin-sensitive Staphylococcus aureus (MSSA) sepsis. Diagnostic and therapeutic difficulties confirming an acute VP crisis in the anuric patient are explored. CASE REPORT A 77-year-old South African woman presented with undifferentiated MSSA sepsis. Despite escalation to intensive care and treatment of her infection, she developed encephalopathy, tetraparesis, autonomic dysfunction, and anuric renal failure, requiring renal replacement therapy. Given her anuric state, novel assays of the dialysate effluent were performed and revealed elevated PBG levels. Xanthochromic cerebrospinal fluid was also obtained. Taken together with confirmatory plasma porphyrin spectrography, an acute VP neurovisceral crisis with multiorgan failure was established. Intravenous heme-arginate combined with extracorporeal filtration via continuous renal replacement therapy and therapeutic plasma exchange were initiated. Inappropriate blood leak detector clamping occurred during extracorporeal filtration due to the presence of porphyrins in the effluent. Despite these aggressive measures, the patient died due to her illness. CONCLUSIONS Progressive neurological compromise, coupled with undifferentiated multiorgan failure, should prompt consideration of an underlying acute porphyric crisis. In anuric porphyria patients, PBG assays of extracorporeal circuit effluents may be of diagnostic value. Effluent PBGs can interfere with the extracorporeal circuit blood leak detector, thereby offering further clinical suspicion of an underlying acute porphyric crisis.

Indexed as

Multiple Organ FailurePorphyria, VariegateAgedFemaleHumansPorphobilinogenStaphylococcal InfectionsPorphobilinogen

Identifiers

PMID40285338
PMCPMC12046175

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Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the OpenQuestion graph.