Evidence map›Paper›PMID 40208077›Full record

ArticleThe journal of international advanced otology2025

Neuro-Otological Manifestations in Patients with a Hemifacial Port-Wine Stain: A Report of 2 Cases.

Stefan Delrue, Rosanne Van Oosterwyck, Tom Cammaert, Philippe Heylbroeck, Stephanie Vanden Bossche, Glen Forton, Marc Lemmerling

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In one paragraph

Article in The journal of international advanced otology, 2025. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Not yet cited in PubMed.

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0citing papers in PubMed
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1 · What the graph read from it

What it found

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The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

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3 · Its place in the literature

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0 citing papers in PubMed.

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4 · The record

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5 · Who and what money

Authors and funding

7 authors.

Stefan DelrueDepartment of Otorhinolaryngology, Head and Neck Surgery, AZ Sint-Lucas, Ghent, Belgium.
Rosanne Van OosterwyckDepartment of Otorhinolaryngology, Head and Neck Surgery, AZ Sint-Lucas, Ghent, Belgium.
Tom CammaertDepartment of Otorhinolaryngology, Head and Neck Surgery, AZ Sint-Lucas, Ghent, Belgium.
Philippe HeylbroeckDepartment of Otorhinolaryngology, Head and Neck Surgery, AZ Sint-Lucas, Ghent, Belgium.
Stephanie Vanden BosscheDepartment of Radiology, AZ Sint-Lucas, Ghent, Belgium.
Glen FortonDepartment of Otorhinolaryngology, Head and Neck Surgery, AZ Delta, Roeselare, Belgium.
Marc LemmerlingDepartment of Radiology, Antwerp University Hospital, Antwerp, Belgium.

Funding

No grant is acknowledged in the PubMed record.

6 · The paper itself

Abstract

A port-wine stain (PWS) or nevus flammeus is a congenital capillary malformation that often affects the skin of the head and neck region. Little is known about neuro-otological manifestations associated with this birthmark. We describe 2 patients with a hemifacial PWS and sensorineural hearing loss, caused by involvement of the internal auditory canal (IAC) and inner ear structures. Case one had a history of sudden vestibular hypofunction, followed by high-frequency sensorineural hearing loss 2 years later. In the second case, the exact onset of the high-frequency hearing loss could not be determined. In both patients, magnetic resonance imaging (MRI) showed dural enhancement of the IAC and a loss of T2 signal intensity of the ipsilateral labyrinth. This report shows that a PWS of the head and neck region may be associated with dural thickening within the IAC and secondary inner ear dysfunction. In patients with this capillary malformation suffering from hearing impairment or balance problems, MRI is warranted to detect involvement of the ipsilateral dura and labyrinth.

Indexed as

Ear, InnerHearing Loss, SensorineuralPort-Wine StainAdultHumansMagnetic Resonance ImagingMaleMiddle Ageddura matermagnetic resonance imagingPort-wine stainsensorineural hearing loss

Identifiers

PMID40208077
PMCPMC12001503

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Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the OpenQuestion graph.