Evidence map›Paper›PMID 40175156›Full record

ReviewEndocrine journal2025

p.M918W, a novel RET germline variant: a case report and literature review of the possible association of multiple endocrine neoplasia type 2B and Charcot-Marie-Tooth disease.

Mami Sato, Rei Kubota, Shinya Uchino, Takayuki Morita, Ryoyu Niikuni, Teruhisa Udagawa, Yoshiya Hagiwara, Miyako Tanaka, Miku Sato, Yuta Tezuka and 6 more

Abstract readCase ReportsReview
In one paragraph

Review in Endocrine journal, 2025. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Not yet cited in PubMed.

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0cells of the map it votes in
0citing papers in PubMed
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1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

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Neither the registry nor the abstract names a trial number. If this is a trial report, that itself is worth knowing.

3 · Its place in the literature

Who cites it

0 citing papers in PubMed.

No citing paper in PubMed yet.

4 · The record

Corrections and comments

PubMed lists nothing against this paper. Absence here is not a guarantee, only a check that was made.

5 · Who and what money

Authors and funding

16 authors.

Mami SatoDepartment of Surgery, Tohoku University Hospital, Sendai, Miyagi 980-8574, Japan.
Rei KubotaHachinohe City Hospital, Hachinohe, Aomori 031-8555, Japan.
Shinya UchinoDepartment of Endocrine Surgery, Noguchi Thyroid Clinic and Hospital Foundation, Beppu, Oita 874-0902, Japan.
Takayuki MoritaDepartment of Surgery, Tohoku University Hospital, Sendai, Miyagi 980-8574, Japan.
Ryoyu NiikuniDepartment of Surgery, Tohoku University Hospital, Sendai, Miyagi 980-8574, Japan.
Teruhisa UdagawaDepartment of Surgery, Suifu Hospital, Mito, Ibaraki 311-4141, Japan.
Yoshiya HagiwaraDepartment of Surgery, Tohoku University Hospital, Sendai, Miyagi 980-8574, Japan.
Miyako TanakaDepartment of Surgery, Tohoku University Hospital, Sendai, Miyagi 980-8574, Japan.
Miku SatoDepartment of Surgery, Tohoku University Hospital, Sendai, Miyagi 980-8574, Japan.
Yuta TezukaDepartment of Diabetes, Metabolism and Endocrinology, Tohoku University Hospital, Sendai, Miyagi 980-8574, Japan.
Kei OmataDepartment of Diabetes, Metabolism and Endocrinology, Tohoku University Hospital, Sendai, Miyagi 980-8574, Japan.
Yoshikiyo OnoDepartment of Diabetes, Metabolism and Endocrinology, Tohoku University Hospital, Sendai, Miyagi 980-8574, Japan.
Kazuhiro HaginoyaDepartment of Pediatric Neurology, Miyagi Children's Hospital, Sendai, Miyagi 989-3126, Japan.
Noriaki NakashimaDepartment of Surgery, Suifu Hospital, Mito, Ibaraki 311-4141, Japan.
Keisei FujimoriDepartment of Surgery, Tohoku University Hospital, Sendai, Miyagi 980-8574, Japan.
Takanori IshidaDepartment of Surgery, Tohoku University Hospital, Sendai, Miyagi 980-8574, Japan.

Funding

No grant is acknowledged in the PubMed record.

6 · The paper itself

Abstract

Multiple endocrine neoplasia type 2B (MEN2B) is a rare autosomal dominant disorder caused by germline pathogenic RET variants. On the other hand, Charcot-Marie-Tooth disease (CMT) is a hereditary neurological disorder, characterized by distal muscle weakness and sensory loss, with approximately 100 identified causative genes. Herein, we report a de novo RET mutation in a patient presenting with clinical features of both MEN2B and CMT. The patient, a 22-year-old woman, had a history of lower limb muscle weakness, with no family history of MEN2B or CMT. The patient was being treated for a thyroid gland neoplasm. Genetic testing of the medullary thyroid carcinoma revealed a previously unreported RET germline variant, p.M918W (RET: c.2752_2753delinsTG, p.Met918Trp). The novel p.M918W RET variant was associated with concurrent MEN2B and CMT. This finding was unexpected as MEN2B typically manifests with distinct features, such as marfanoid habitus and mucosal neuromas, but not with muscle weakness, as seen in CMT. Based on this finding, the plausible role of the p.M918W mutation as a shared pathway for both MEN2B and CMT warrants further investigation.

Indexed as

Charcot-Marie-Tooth DiseaseGerm-Line MutationMultiple Endocrine Neoplasia Type 2bProto-Oncogene Proteins c-retCarcinoma, NeuroendocrineFemaleHumansThyroid NeoplasmsYoung AdultProto-Oncogene Proteins c-retRET protein, humanCharcot–Marie–Tooth diseaseMedullary thyroid carcinomaMultiple endocrine neoplasia type 2BRETRET variant

Identifiers

PMID40175156
PMCPMC12260187

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Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the OpenQuestion graph.