Evidence map›Paper›PMID 40051946›Full record

ArticleCureus2025

Liver Transplantation as a Definitive Treatment for Homozygous Protein C Deficiency.

Juwairiya Syed Iqbaluddin, Saista Asif Amin, Hanan Fawzy Nazir Abouelkhel, Johns Shaji Mathew, Gourab Sen, Rehan Saif

Abstract readCase Reports
In one paragraph

Article in Cureus, 2025. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Cited by 1 paper.

0numbers the graph read from it
0cells of the map it votes in
1citing papers in PubMed
–field-weighted citation impact
1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

Trials whose registry record cites this paper, or whose number appears in the abstract. A trial that started after this paper was published is citing it as background, not reporting it.

Neither the registry nor the abstract names a trial number. If this is a trial report, that itself is worth knowing.

3 · Its place in the literature

Who cites it

1 citing paper in PubMed.

  1. Article
4 · The record

Corrections and comments

PubMed lists nothing against this paper. Absence here is not a guarantee, only a check that was made.

5 · Who and what money

Authors and funding

6 authors.

Juwairiya Syed IqbaluddinPediatrics, Al Qassimi Women's and Children's Hospital, Sharjah, ARE.
Saista Asif AminPediatric Gastroenterology, American Hospital Dubai, Dubai, ARE.
Hanan Fawzy Nazir AbouelkhelPediatric Hematology, Al Qassimi Women's and Children's Hospital, Sharjah, ARE.
Johns Shaji MathewHepatobiliary and Abdominal Multi-organ Transplant Surgery, Burjeel Medical City, Abu Dhabi, ARE.
Gourab SenHepatobiliary and Abdominal Multi-organ Transplant Surgery, Burjeel Medical City, Abu Dhabi, ARE.
Rehan SaifHepatobiliary and Abdominal Multi-organ Transplant Surgery, Burjeel Medical City, Abu Dhabi, ARE.

Funding

No grant is acknowledged in the PubMed record.

6 · The paper itself

Abstract

Protein C is a vitamin K-dependent anticoagulant glycoprotein that inhibits activated factors V and VIII once activated by thrombin while promoting fibrinolysis. Patients with homozygous protein C deficiency generally present shortly after birth with purpura fulminans, retinal hemorrhage, and signs of the central nervous system or renal thrombosis. This case reports the first case of homozygous protein C deficiency in the UAE successfully treated with liver transplantation. This article aims to emphasize the importance of early diagnosis of neonatal purpura fulminans based on clinical presentation and to maintain a high index of suspicion for protein C deficiency. It seeks to illustrate that liver transplantation can effectively restore protein C activity, offering a life-saving treatment for a condition that would otherwise be devastating. Additionally, in resource-limited settings, the article highlights the potential use of fresh frozen plasma (FFP) as an alternative to protein C concentrate for supporting protein C levels during the perioperative period. We present an eight-year-old female who was diagnosed with protein C deficiency at birth in her home country following the onset of purpura fulminans. She received regular FFP transfusions but continued to experience complications such as blindness, leg contractures, and infections despite treatments with protein C concentrate and warfarin. Seeking further care, she was evaluated in the UAE for liver transplantation, a potentially curative treatment for this disorder. After being placed on the national transplant waiting list, the patient underwent a successful liver transplantation from a deceased donor. Perioperative management included careful monitoring of protein C levels and blood products to prevent thrombotic and bleeding complications. Her protein C activity normalized post-transplant, and there were no thrombotic events. This case highlights the potential of liver transplantation as a definitive cure for homozygous protein C deficiency. In conclusion, liver transplantation should be considered as a definitive treatment for children with homozygous protein C deficiency who experience recurrent thrombotic events despite replacement therapy and for those with severely impaired quality of life due to the disease itself. The decision to proceed with transplantation should be made with careful consideration of the patient's long-term quality of life and the balance between transplant-related risks and the benefits of avoiding continuous anticoagulation therapy.

Indexed as

fresh frozen plasmahomozygous protein c deficiencyliver transplantationpurpura fulminansretinal haemorrhage

Identifiers

PMID40051946
PMCPMC11884642

What OpenQuestion holds

Textmetadata
LicenceCC BY
Read underepoch 390

Registered trials

None linked

Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the OpenQuestion graph.