Evidence map›Paper›PMID 39976362›Full record

ReviewEpilepsia open2025

GATAD2B-related developmental and epileptic encephalopathy (DEE): Extending the epilepsy phenotype and a literature appraisal.

Giovanna Scorrano, Giulia Barcia, Jérôme Champ, Thomas Courtin, Nathalie Boddaert, Anna Kaminska, Nicole Chemaly, Rima Nabbout

Abstract readCase ReportsReview
In one paragraph

Review in Epilepsia open, 2025. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Cited by 1 paper.

0numbers the graph read from it
0cells of the map it votes in
1citing papers in PubMed
–field-weighted citation impact
1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

Trials whose registry record cites this paper, or whose number appears in the abstract. A trial that started after this paper was published is citing it as background, not reporting it.

Neither the registry nor the abstract names a trial number. If this is a trial report, that itself is worth knowing.

3 · Its place in the literature

Who cites it

1 citing paper in PubMed.

  1. Review
4 · The record

Corrections and comments

PubMed lists nothing against this paper. Absence here is not a guarantee, only a check that was made.

5 · Who and what money

Authors and funding

8 authors.

Giovanna ScorranoDepartment of Pediatric Neurology, Reference Centre for Rare Epilepsies, Necker Enfants Malades University Hospital, AP-HP, Université Paris Cité, Paris, France.ORCID https://orcid.org/0009-0007-7504-0540
Giulia BarciaDepartment of Genetics, Necker Enfants Malades University Hospital, AP-HP, Université Paris Cité, Paris, France.ORCID https://orcid.org/0000-0001-6657-5040
Jérôme ChampLaboratoire de Biologie Médicale Multi-Sites SeqOIA Assistance-Publique, Paris, France.
Thomas CourtinDepartment of Genetics, Necker Enfants Malades University Hospital, AP-HP, Université Paris Cité, Paris, France.
Nathalie BoddaertDepartment of Pediatric Radiology, Necker Enfants Malades Hospital, AP-HP, Université Paris Cité, Paris, France.
Anna KaminskaClinical Neurophysiology Department, Necker Enfants Malades University Hospital, AP-HP, Université Paris Cité, Paris, France.ORCID https://orcid.org/0000-0003-3805-6651
Nicole ChemalyDepartment of Pediatric Neurology, Reference Centre for Rare Epilepsies, Necker Enfants Malades University Hospital, AP-HP, Université Paris Cité, Paris, France.
Rima NabboutDepartment of Pediatric Neurology, Reference Centre for Rare Epilepsies, Necker Enfants Malades University Hospital, AP-HP, Université Paris Cité, Paris, France.ORCID https://orcid.org/0000-0001-5877-4074

Funding

No grant is acknowledged in the PubMed record.

6 · The paper itself

Abstract

Heterozygous pathogenic variants in GATAD2B gene have been related to the GATAD2B-associated neurodevelopmental disorders (GAND) characterized by neurodevelopmental delay with predominant language impairment, infantile hypotonia, macrocephaly, ophthalmological abnormalities, and dysmorphic facial features with nonspecific findings on brain magnetic resonance imaging (MRI). Occasionally, affected individuals exhibit drug responsive epilepsy, psychiatric disorders, and other extra-neurological comorbidities. We report a patient carrying a de novo heterozygous missense variant in GATAD2B gene. She presents a developmental and epileptic encephalopathy (DEE) with drug-resistant atypical absences. An extensive review of the literature did not show any similar phenotype. Our report broadens the electroclinical spectrum related to GATAD2B pathogenic variants and supports the inclusion of this monogenic etiology among the genetic causes of epilepsy with drug-resistant atypical absences, a group with few known genetic etiologies. PLAIN LANGUAGE SUMMARY: We describe a patient with drug-resistant atypical absences caused by a pathogenic variant in the GATAD2B gene. Mutations in the GATAD2B gene should be considered among the rare monogenic causes of atypical absences.

Indexed as

Developmental DisabilitiesDrug Resistant EpilepsyEpilepsy, AbsenceNeurodevelopmental DisordersAdolescentElectroencephalographyEpilepsyFemaleHumansMutation, MissensePhenotypeepilepsyGATAD2Bheterozygous variantsneurodevelopmental delay

Identifiers

PMID39976362
PMCPMC12014912

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Registered trials

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Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the OpenQuestion graph.