Evidence map›Paper›PMID 39735239›Full record

ArticleJournal of otology2024

Thiamine responsive megaloblastic Anemia and deafness: A rare case of Roger's syndrome with successful hearing rehabilitation by cochlear implantation.

Hetal Marfatia, Anoushka Sahai, Kartik Narkhede, Monankita Sharma

Abstract read
In one paragraph

Article in Journal of otology, 2024. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Cited by 2 papers.

0numbers the graph read from it
0cells of the map it votes in
2citing papers in PubMed
–field-weighted citation impact
1 · What the graph read from it

What it found

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The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

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3 · Its place in the literature

Who cites it

2 citing papers in PubMed.

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4 · The record

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5 · Who and what money

Authors and funding

4 authors.

Hetal MarfatiaDepartment of ENT and Head-Neck Surgery, Seth G.S. Medical College and KEM Hospital, Acharya Donde Marg, Parel, Mumbai, Maharashtra, 400012, India.
Anoushka SahaiDepartment of ENT and Head-Neck Surgery, Seth G.S. Medical College and KEM Hospital, Acharya Donde Marg, Parel, Mumbai, Maharashtra, 400012, India.
Kartik NarkhedeDepartment of ENT and Head-Neck Surgery, Seth G.S. Medical College and KEM Hospital, Acharya Donde Marg, Parel, Mumbai, Maharashtra, 400012, India.
Monankita SharmaDepartment of ENT and Head-Neck Surgery, Seth G.S. Medical College and KEM Hospital, Acharya Donde Marg, Parel, Mumbai, Maharashtra, 400012, India.

Funding

No grant is acknowledged in the PubMed record.

6 · The paper itself

Abstract

Thiamine responsive megaloblastic anemia (TRMA), also known as Roger's syndrome, is an exceptionally rare autosomal recessive disorder stemming from mutations in the SLC19A2 gene responsible for encoding a thiamine carrier protein. This syndrome manifests as the classic triad of megaloblastic anemia, sensorineural hearing loss, and diabetes mellitus. Here, we present the case of a one-and-a-half-year-old male infant born to non-consanguineous parents in India, a region where TRMA cases are seldom reported. At five months of age, the child exhibited the characteristic symptoms, prompting immediate treatment involving thiamine therapy, insulin administration, and blood transfusions. Notably, the child exhibited significant improvement in all aspects except for hearing loss, which conventional hearing aids failed to alleviate. However, following a cochlear implant procedure conducted within a few months, the child regained hearing abilities. This case underscores the importance of early recognition and intervention in the form of cochlear implant, demonstrating the potential to reverse TRMA symptoms and provide affected individuals with a substantially improved quality of life.

Indexed as

Cochlear implantDiabetic ketoacidosisHearing lossMegaloblastic anemiaRoger's syndrome

Identifiers

PMID39735239
PMCPMC11681787

What OpenQuestion holds

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LicenceCC BY-NC-ND
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Registered trials

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Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the OpenQuestion graph.