Evidence map›Paper›PMID 38778080›Full record

ArticleEuropean journal of human genetics : EJHG2024

Comparison of the ABC and ACMG systems for variant classification.

Gunnar Houge, Eirik Bratland, Ingvild Aukrust, Kristian Tveten, Gabrielė Žukauskaitė, Ivona Sansovic, Alejandro J Brea-Fernández, Karin Mayer, Teija Paakkola, Caoimhe McKenna and 38 more

Abstract readComparative Study
In one paragraph

Article in European journal of human genetics : EJHG, 2024. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Cited by 13 papers, 1 of them a synthesis that pooled it.

0numbers the graph read from it
0cells of the map it votes in
13citing papers in PubMed, 1 pooled it
–field-weighted citation impact
1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

Trials whose registry record cites this paper, or whose number appears in the abstract. A trial that started after this paper was published is citing it as background, not reporting it.

Neither the registry nor the abstract names a trial number. If this is a trial report, that itself is worth knowing.

3 · Its place in the literature

Who cites it

13 citing papers in PubMed, 1 synthesis or guideline pooled it.

  1. Guideline
  2. The Tyrolean FounderBiomolecules · 2026
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  5. Review
  6. Genetic analysis of neurodegenerative diseases.The Journal of clinical investigation · 2026
    Review
  7. Article
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  10. Review
  11. Review
  12. Review
  13. Hitting the heights with CiteScore.European journal of human genetics : EJHG · 2024
    Article
4 · The record

Corrections and comments

PubMed lists nothing against this paper. Absence here is not a guarantee, only a check that was made.

5 · Who and what money

Authors and funding

48 authors.

Gunnar HougeDepartment of Medical Genetics, Haukeland University Hospital, Bergen, Norway. gunnar.houge@helse-bergen.no.ORCID 0000-0002-6102-1513
Eirik BratlandDepartment of Medical Genetics, Haukeland University Hospital, Bergen, Norway.
Ingvild AukrustDepartment of Medical Genetics, Haukeland University Hospital, Bergen, Norway.
Kristian TvetenDepartment of Medical Genetics, Telemark Hospital Trust, Skien, Norway.ORCID 0000-0003-1316-5843
Gabrielė ŽukauskaitėDepartment of Human and Medical Genetics, Institute of Biomedical Sciences, Faculty of Medicine, Vilnius University, Vilnius, Lithuania.ORCID 0000-0003-1726-5825
Ivona SansovicDepartment of Medical and Laboratory Genetics, Endocrinology and Diabetology, Childrens' Hospital Zagreb, University of Zagreb School of Medicine, Zagreb, Croatia.ORCID 0000-0002-9325-0847
Alejandro J Brea-FernándezGrupo de Medicina Xenómica, Universidade de Santiago de Compostela, CIBERER), Santiago de Compostela, Spain.ORCID 0000-0003-1527-471X
Karin MayerCenter for Human Genetics and Laboratory Diagnostics, MVZ Martinsried GmbH, Martinsried, Germany.
Teija PaakkolaNordlab Wellbeing Service Group, Genetics Laboratory, Oulu, Finland.ORCID 0000-0003-4788-5822
Caoimhe McKennaNorthern Ireland Regional Molecular Diagnostic Service, Belfast, Northern Ireland.
William WrightNorthern Ireland Regional Molecular Diagnostic Service, Belfast, Northern Ireland.
Milica Keckarevic MarkovicCenter for Applied and Forensic Molecular Genetics, Faculty of Biology, University of Belgrade, Belgrade, Serbia.ORCID 0000-0001-9866-9439
Dorte L LildballeDepartment of Molecular Medicine, Aarhus University Hospital, Aarhus, Denmark.ORCID 0000-0003-0223-1673
Michal KonecnyLaboratory of Genomic Medicine, GHC GENETICS SK, Bratislava, Slovakia.
Thomas SmolInstitut de Genetique Medicale-CHU Lille, Lille, France.
Pia AlhopuroHUS Diagnostic Center, Laboratory of Genetics, University of Helsinki and Helsinki University Hospital, Helsinki, Finland.ORCID 0000-0001-5745-0449
Estelle Arnaud GouttenoireMEDISYN Genetics, Chemin d'Entre-Bois 21, Lausanne, Switzerland.
Katharina ObeidMolecular Diagnostics, Institute of Human Genetics, University Hospital Heidelberg, Heidelberg, Germany.
Albena TodorovaGenetic Medico-Diagnostic Laboratory "Genica" and Genome Center Bulgaria, Sofia, Bulgaria.
Milena JankovicNeurology Clinic UCCS, Faculty of Medicine, University of Belgrade, Belgrade, Serbia.ORCID 0000-0002-3939-9739
Joanna M LubienieckaHumangenetik, Ruhr-Universität Bochum, Bochum, Germany.
Maja StojiljkovicInstitute of Molecular Genetics and Genetic Engineering, University of Belgrade, Belgrade, Serbia.
Marie-Pierre BuisineMolecular Oncogenetics, Department of Biochemistry and Molecular Biology, Lille University Hospital, Lille, France.
Bjørn Ivar HaukanesDepartment of Medical Genetics, Haukeland University Hospital, Bergen, Norway.
Marie LoransDepartment of Clinical Genetics, Aarhus University Hospital, Aarhus, Denmark.ORCID 0009-0009-0016-3516
Hanno RoomereDepartment of laboratory genetics, Genetics and Personalized Medicine Clinic, Tartu University Hospital, Tartu, Estonia.
François M PetitDepartment of Oncopharmacology, Centre Antoine Lacassagne, Nice, France.ORCID 0000-0002-6506-8060
Maria K HaanpääDepartment of Genomics, Turku University Hospital, Turku, Finland.ORCID 0000-0003-3731-863X
Claire BeneteauCHU Bordeaux, Service de Génétique Médicale, F-33000, Bordeaux, France.ORCID 0000-0002-1682-523X
Belén PérezGenetics Department of CEDEM, Universidad Autónoma de Madrid, Madrid, Spain.
Dijana Plaseska-KaranfilskaResearch Centre for Genetic Engineering and Biotechnology "Georgi D. Efremov", Macedonian Academy of Sciences and Arts, Skopje, North Macedonia.ORCID 0000-0001-8877-2416
Matthias RathInstitute for Molecular Medicine, MSH Medical School Hamburg, Hamburg, Germany.
Nico FuhrmannInstitute of Human Genetics, University of Cologne, Cologne, Germany.ORCID 0000-0002-3302-3669
Bibiana I FerreiraGENELAB by ABC, Faro, Portugal.
Coralea StephanouMolecular Genetics Thalassemia Department, The Cyprus Institute of Neurology and Genetics, Nicosia, Cyprus.ORCID 0000-0002-2546-6478
Wenche SjursenDepartment of Medical Genetics, St Olavs Hospital, Trondheim, Norway.
Aleš MaverClinical Institute of Genomic Medicine, Ljubljana, Slovenia.
Cécile RouzierDepartment of Medical Genetics, National Centre for Mitocondrial Diseases, CHU de NICE, Université Côte d'Azur, Nice, France.ORCID 0000-0002-2969-1904
Adela Chirita-EmandiDepartment of Microscopic Morphology Genetics Discipline, Center of Genomic Medicine, "Victor Babes" University of Medicine and Pharmacy Timisoara, Timisoara, Romania.ORCID 0000-0001-7554-4625
João GonçalvesHuman Genetics Department, National Institute of Health Dr Ricardo Jorge, Lisbon, Portugal.
Wei Cheng David KuekMolecular Diagnosis Centre, Department of Laboratory Medicine, National University Hospital, Kent Ridge, Singapore.ORCID 0009-0005-5992-6312
Martin BrolyLaboratory of Rare and Autoinflammatory Genetic Diseases, Department of Genetics-LBM, Montpellier University Hospital, Montpellier, France.
Lonneke Haer-WigmanDepartment of Human Genetics, Radboud University Medical Center, Nijmegen, The Netherlands.
Meow-Keong ThongGenetics and Metabolism Unit, Department of Pediatrics, Faculty of Medicine, University of Malaya, Kuala Lumpur, Malaysia.ORCID 0000-0002-7288-7910
Sok-Kun TaeGenetics and Metabolism Unit, Department of Pediatrics, Faculty of Medicine, University of Malaya, Kuala Lumpur, Malaysia.ORCID 0009-0002-7236-1430
Michaela HyblovaDepartment of Genetics, Medirex, Bratislava, Slovakia.ORCID 0000-0001-6519-4967
Johan T den DunnenDepartment of Human Genetics, Leiden University Medical Center, Leiden, The Netherlands.
Andreas LanerMedizinisch Genetisches Zentrum (MGZ) München, Munich, Germany.ORCID 0000-0003-4596-7293

Funding

No grant is acknowledged in the PubMed record.

6 · The paper itself

Abstract

The ABC and ACMG variant classification systems were compared by asking mainly European clinical laboratories to classify variants in 10 challenging cases using both systems, and to state if the variant in question would be reported as a relevant result or not as a measure of clinical utility. In contrast to the ABC system, the ACMG system was not made to guide variant reporting but to determine the likelihood of pathogenicity. Nevertheless, this comparison is justified since the ACMG class determines variant reporting in many laboratories. Forty-three laboratories participated in the survey. In seven cases, the classification system used did not influence the reporting likelihood when variants labeled as "maybe report" after ACMG-based classification were included. In three cases of population frequent but disease-associated variants, there was a difference in favor of reporting after ABC classification. A possible reason is that ABC step C (standard variant comments) allows a variant to be reported in one clinical setting but not another, e.g., based on Bayesian-based likelihood calculation of clinical relevance. Finally, the selection of ACMG criteria was compared between 36 laboratories. When excluding criteria used by less than four laboratories (<10%), the average concordance rate was 46%. Taken together, ABC-based classification is more clear-cut than ACMG-based classification since molecular and clinical information is handled separately, and variant reporting can be adapted to the clinical question and phenotype. Furthermore, variants do not get a clinically inappropriate label, like pathogenic when not pathogenic in a clinical context, or variant of unknown significance when the significance is known.

Indexed as

Genetic VariationGenetic TestingHumans

Identifiers

PMID38778080
PMCPMC11219933

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