Evidence map›Paper›PMID 38619706›Full record

ArticleBiochemical genetics2025

Broadening the Phenotype and Genotype Spectrum of Glycogen Storage Disease by Unraveling Novel Variants in an Iranian Patient Cohort.

Parinaz Moghimi, Farzad Hashemi-Gorji, Sanaz Jamshidi, Sahand Tehrani Fateh, Shadab Salehpour, Hossein Sadeghi, Fatemeh Norouzi Rostami, Reza Mirfakhraie, Mohammad Miryounesi, Mohammad-Reza Ghasemi

Abstract read
PubMed Publisher
In one paragraph

Article in Biochemical genetics, 2025. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Cited by 1 paper, 1 of them a synthesis that pooled it.

0numbers the graph read from it
0cells of the map it votes in
1citing papers in PubMed, 1 pooled it
0.5field-weighted citation impact, top 37% of its field
1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

Trials whose registry record cites this paper, or whose number appears in the abstract. A trial that started after this paper was published is citing it as background, not reporting it.

Neither the registry nor the abstract names a trial number. If this is a trial report, that itself is worth knowing.

3 · Its place in the literature

Who cites it

1 citing paper in PubMed, 1 synthesis or guideline pooled it, 1 citations in OpenAlex.

  1. Pooled it
4 · The record

Corrections and comments

PubMed lists nothing against this paper. Absence here is not a guarantee, only a check that was made.

5 · Who and what money

Authors and funding

10 authors at 4 institutions in 1 country.

Parinaz MoghimiCenter for Comprehensive Genetic Services, Shahid Beheshti University of Medical Sciences, Tehran, Iran.ORCID http://orcid.org/0009-0007-7264-7793
Farzad Hashemi-GorjiGenomic Research Center, Shahid Beheshti University of Medical Sciences, Tehran, Iran.ORCID http://orcid.org/0000-0002-9996-9406
Sanaz JamshidiCenter for Comprehensive Genetic Services, Shahid Beheshti University of Medical Sciences, Tehran, Iran.ORCID http://orcid.org/0000-0002-3937-6043
Sahand Tehrani FatehSchool of Medicine, Tehran University of Medical Sciences (TUMS), Tehran, Iran.ORCID http://orcid.org/0009-0002-8903-2713
Shadab SalehpourDepartment of Pediatrics, Clinical Research Development Unit, Loghman Hakim Hospital, Shahid Beheshti University of Medical Sciences, Tehran, Iran.ORCID http://orcid.org/0000-0002-0277-809X
Hossein SadeghiDepartment of Medical Genetics, Faculty of Medicine, Shahid Beheshti University of Medical Sciences, Tehran, Iran.ORCID http://orcid.org/0000-0001-9599-6151
Fatemeh Norouzi RostamiDepartment of Chemistry, Faculty of Science, Ferdowsi University of Mashhad, Mashhad, Iran.
Reza MirfakhraieDepartment of Medical Genetics, Faculty of Medicine, Shahid Beheshti University of Medical Sciences, Tehran, Iran.ORCID http://orcid.org/0000-0003-1709-8975
Mohammad MiryounesiCenter for Comprehensive Genetic Services, Shahid Beheshti University of Medical Sciences, Tehran, Iran. miryounesi@gmail.com.ORCID http://orcid.org/0000-0003-4705-3794
Mohammad-Reza GhasemiCenter for Comprehensive Genetic Services, Shahid Beheshti University of Medical Sciences, Tehran, Iran. ghasemimr891@gmail.com.ORCID http://orcid.org/0000-0002-3183-5495
Shahid Beheshti University of Medical Sciences · IRFerdowsi University of Mashhad · IRIslamic Azad University Medical Branch of Tehran · IRTehran University of Medical Sciences · IR

Funding

No grant is acknowledged in the PubMed record.

6 · The paper itself

Abstract

Glycogen storage diseases (GSDs) are a group of rare inherited metabolic disorders characterized by clinical, locus, and allele heterogeneity. This study aims to investigate the phenotype and genotype spectrum of GSDs in a cohort of 14 families from Iran using whole-exome sequencing (WES) and variant analysis. WES was performed on 14 patients clinically suspected of GSDs. Variant analysis was performed to identify genetic variants associated with GSDs. A total of 13 variants were identified, including six novel variants, and seven previously reported pathogenic variants in genes such as AGL, G6PC, GAA, PYGL, PYGM, GBE1, SLC37A4, and PHKA2. Most types of GSDs observed in the cohort were associated with hepatomegaly, which was the most common clinical presentation. This study provides valuable insights into the phenotype and genotype spectrum of GSDs in a cohort of Iranian patients. The identification of novel variants adds to the growing body of knowledge regarding the genetic landscape of GSDs and has implications for genetic counseling and future therapeutic interventions. The diverse nature of GSDs underscores the need for comprehensive genetic testing methods to improve diagnostic accuracy. Continued research in this field will enhance our understanding of GSDs, ultimately leading to improved management and outcomes for individuals affected by these rare metabolic disorders.

Indexed as

Glycogen Storage DiseaseMutationAdolescentAdultChildChild, PreschoolCohort StudiesExome SequencingFemaleGenotypeHumansInfantIranMalePhenotypeGenetic counselingGlycogen storage diseases (GSDs)Inherited metabolic disordersNovel VariantsWhole-Exome Sequencing (WES)

Identifiers

PMID38619706
OpenAlexW4394808475

What OpenQuestion holds

Textmetadata
Read underepoch 390

Registered trials

None linked

Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the OpenQuestion graph.