Evidence map›Paper›PMID 38186849›Full record

ArticleJIMD reports2024

Psychosocial issues and coping strategies in families affected by long-chain fatty acid oxidation disorders.

Maren Thiel, Sven F Garbade, Stefanie Rosenbaum-Fabian, Ute Spiekerkoetter, Sarah C Grünert

Open access · goldAbstract read
In one paragraph

Article in JIMD reports, 2024. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Cited by 6 papers.

0numbers the graph read from it
0cells of the map it votes in
6citing papers in PubMed
0.6field-weighted citation impact, top 32% of its field
1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

Trials whose registry record cites this paper, or whose number appears in the abstract. A trial that started after this paper was published is citing it as background, not reporting it.

Neither the registry nor the abstract names a trial number. If this is a trial report, that itself is worth knowing.

3 · Its place in the literature

Who cites it

6 citing papers in PubMed, 3 citations in OpenAlex.

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4 · The record

Corrections and comments

PubMed lists nothing against this paper. Absence here is not a guarantee, only a check that was made.

5 · Who and what money

Authors and funding

5 authors at 2 institutions in 1 country.

Maren ThielDepartment of General Pediatrics, Adolescent Medicine and Neonatology Faculty of Medicine, University Medical Center, University of Freiburg Freiburg Germany.
Sven F GarbadeDivision of Pediatric Neurology and Metabolic Medicine, Center for Pediatric and Adolescent Medicine University Hospital Heidelberg Heidelberg Germany.
Stefanie Rosenbaum-FabianDepartment of General Pediatrics, Adolescent Medicine and Neonatology Faculty of Medicine, University Medical Center, University of Freiburg Freiburg Germany.
Ute SpiekerkoetterDepartment of General Pediatrics, Adolescent Medicine and Neonatology Faculty of Medicine, University Medical Center, University of Freiburg Freiburg Germany.
Sarah C GrünertDepartment of General Pediatrics, Adolescent Medicine and Neonatology Faculty of Medicine, University Medical Center, University of Freiburg Freiburg Germany.ORCID https://orcid.org/0000-0001-5986-0468
University of Freiburg · DEHeidelberg University · DE

Funding

No grant is acknowledged in the PubMed record.

6 · The paper itself

Abstract

Long-chain fatty acid oxidation disorders (lcFAODs) are associated with a high disease burden due to both the risk of metabolic decompensation as well as chronic, partly irreversible complications in some. Little research has been performed on the impact of these disorders on the daily life of parents and caregivers. We performed a web-based questionnaire study among parents/caregivers of patients affected with lcFAODs. The questionnaire focused on challenges at different ages of the child, on disease management issues, schooling, family and social life as well as the parental job situation, and their overall attitude toward the disease and the future life of their child. Data were collected from parents/caregivers of 63 patients (87 respondents, 63% mothers, 36% fathers) with lcFAODs (median age of patients 8.0 years, range 0-25 years, long-chain 3-hydrocyacyl-CoA dehydrogenase deficiency 40%, mitochondrial trifunctional protein deficiency 14%, very long-chain acyl-CoA dehydrogenase deficiency 41%, carnitine palmitoyltransferase 2 deficiency 5%). The overall disease burden of parents was considered highest during infancy and decreased with increasing age of their child. More than one third of parents were afraid that their child's disease might have an impact on his/her career choice and adult life. Negative effects of the child's disease on the job situation and career development were more commonly reported by mothers compared to fathers. Although the majority of parents considered their child's metabolic disorder a severe disease, most parents had a positive attitude toward their child's disease and seemed to cope well with their situation.

Indexed as

copingdisease burdenfatty acid oxidation defectsfatty acid oxidation disordersquality of life

Identifiers

PMID38186849
PMCPMC10764200
OpenAlexW4389348364

What OpenQuestion holds

Textmetadata
LicenceCC BY
Read underepoch 390

Registered trials

None linked

Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the OpenQuestion graph.