Evidence map›Paper›PMID 38137045›Full record

ReviewGenes2023

Expanding Genotype/Phenotype Correlation in 2p11.2-p12 Microdeletion Syndrome.

Alessandra Ferrario, Nijas Aliu, Claudine Rieubland, Sébastian Vuilleumier, Hilary M Grabe, Pascal Escher

Open access · goldAbstract readCase ReportsReview
In one paragraph

Review in Genes, 2023. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Cited by 1 paper.

0numbers the graph read from it
0cells of the map it votes in
1citing papers in PubMed
0.3field-weighted citation impact, top 30% of its field
1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

Trials whose registry record cites this paper, or whose number appears in the abstract. A trial that started after this paper was published is citing it as background, not reporting it.

Neither the registry nor the abstract names a trial number. If this is a trial report, that itself is worth knowing.

3 · Its place in the literature

Who cites it

1 citing paper in PubMed, 1 citations in OpenAlex.

  1. Article
4 · The record

Corrections and comments

PubMed lists nothing against this paper. Absence here is not a guarantee, only a check that was made.

5 · Who and what money

Authors and funding

6 authors at 2 institutions in 1 country.

Alessandra FerrarioDepartment of Ophthalmology, Inselspital, Bern University Hospital, University of Bern, 3010 Bern, Switzerland.
Nijas AliuDepartment of Human Genetics, Inselspital, Bern University Hospital, University of Bern, 3010 Bern, Switzerland.
Claudine RieublandDepartment of Human Genetics, Inselspital, Bern University Hospital, University of Bern, 3010 Bern, Switzerland.
Sébastian VuilleumierDepartment of Ophthalmology, Inselspital, Bern University Hospital, University of Bern, 3010 Bern, Switzerland.
Hilary M GrabeDepartment of Ophthalmology, Inselspital, Bern University Hospital, University of Bern, 3010 Bern, Switzerland.
Pascal EscherDepartment of Ophthalmology, Inselspital, Bern University Hospital, University of Bern, 3010 Bern, Switzerland.
University Hospital of Bern · CHUniversity of Bern · CH

Funding

No grant is acknowledged in the PubMed record.

6 · The paper itself

Abstract

Chromosomal abnormalities on the short arm of chromosome 2 in the region p11.2 have been associated with developmental delay, intellectual disability, facial anomalies, abnormal ears, skeletal and genital malformations. Here we describe a patient with a de novo interstitial heterozygous microdeletion on the short arm of chromosome 2 in the region p11.2-p12. He presents with facial dysmorphism characterized by a broad and low root of the nose and low-set protruding ears. Clinical examinations during follow-up visits revealed congenital pendular nystagmus, decreased visual acuity and psychomotor development disorder including intellectual disability. The heterozygous 5 Mb-microdeletion was characterized by an array CGH (Comparative Genomic Hybridization) analysis. In the past two decades, nine patients with microdeletions in this region have been identified by array CGH analysis and were reported in the literature. All these patients show psychomotor development disorder and outer and/or inner ear anomalies. In addition, most of the patients have mild to severe intellectual disability and show facial malformations. We reviewed the literature on PubMed and OMIM using the gene/loci names as search terms in an attempt to identify correlations between genes located within the heterozygous microdeletion and the clinical phenotype of the patient, in order to define a recognizable phenotype for the 2p11.2p12 microdeletion syndrome. We discuss additional symptoms that are not systematically present in all patients and contribute to a heterogeneous clinical presentation of this microdeletion syndrome.

Indexed as

Intellectual DisabilityChromosome DeletionComparative Genomic HybridizationGenotypeHumansMalePhenotypechromosome 2congenital ear anomaliesELMOD3facial malformationsFOXI3microdeletionneurodevelopmental disorderPOLR1AREEP1

Identifiers

PMID38137045
PMCPMC10742694
OpenAlexW4389894241

What OpenQuestion holds

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LicenceCC BY
Read underepoch 390

Registered trials

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Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the OpenQuestion graph.