Evidence map›Paper›PMID 37835050›Full record

ReviewJournal of clinical medicine2023

Lysinuric Protein Intolerance and Its Nutritional and Multisystemic Challenges in Pregnancy: A Case Report and Literature Review.

Adriana Pané, Camila Milad, Marta Santana-Domínguez, Núria Baños, Cristina Borras-Novell, Gerard Espinosa, Laura Magnano, Meritxell Nomdedeu, Pedro Juan Moreno-Lozano, Frederic Cofan and 8 more

Open access · goldAbstract readReview
In one paragraph

Review in Journal of clinical medicine, 2023. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Cited by 4 papers.

0numbers the graph read from it
0cells of the map it votes in
4citing papers in PubMed
0.7field-weighted citation impact, top 26% of its field
1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

Trials whose registry record cites this paper, or whose number appears in the abstract. A trial that started after this paper was published is citing it as background, not reporting it.

Neither the registry nor the abstract names a trial number. If this is a trial report, that itself is worth knowing.

3 · Its place in the literature

Who cites it

4 citing papers in PubMed, 3 citations in OpenAlex.

  1. Article
  2. Article
  3. Review
  4. Article
4 · The record

Corrections and comments

PubMed lists nothing against this paper. Absence here is not a guarantee, only a check that was made.

5 · Who and what money

Authors and funding

18 authors at 3 institutions in 2 countries.

Adriana PanéEndocrinology and Nutrition Department, Hospital Clínic, Villarroel 170, 08036 Barcelona, Spain.ORCID 0000-0002-7810-1827
Camila MiladEndocrinology and Nutrition Department, Hospital Clínic, Villarroel 170, 08036 Barcelona, Spain.ORCID 0000-0001-7140-4297
Marta Santana-DomínguezNeonatology Department, BCNatal (Barcelona Center for Fetal and Neonatal Medicine), Hospital Clínic, Villarroel 170, 08036 Barcelona, Spain.
Núria BañosNeonatology Department, BCNatal (Barcelona Center for Fetal and Neonatal Medicine), Hospital Clínic, Villarroel 170, 08036 Barcelona, Spain.ORCID 0000-0001-7022-5270
Cristina Borras-NovellNeonatology Department, BCNatal (Barcelona Center for Fetal and Neonatal Medicine), Hospital Clínic, Villarroel 170, 08036 Barcelona, Spain.
Gerard EspinosaFundació Clínic per la Recerca Biomèdica (FCR), Institut d'Investigacions Biomèdiques August Pi Sunyer (IDIBAPS), 08036 Barcelona, Spain.ORCID 0000-0003-1336-0163
Laura MagnanoFundació Clínic per la Recerca Biomèdica (FCR), Institut d'Investigacions Biomèdiques August Pi Sunyer (IDIBAPS), 08036 Barcelona, Spain.
Meritxell NomdedeuDepartment of Hematology, Hospital Clínic, Villarroel 170, 08036 Barcelona, Spain.
Pedro Juan Moreno-LozanoAdult Inborn Errors of Metabolism Unit, Hospital Clínic, Villarroel 170, 08036 Barcelona, Spain.ORCID 0000-0002-5501-5272
Frederic CofanRenal Transplantation and Nephrology Department, Hospital Clínic, Villarroel 170, 08036 Barcelona, Spain.ORCID 0000-0003-4163-9620
Mercè PlaceresAdult Inborn Errors of Metabolism Unit, Hospital Clínic, Villarroel 170, 08036 Barcelona, Spain.
Rosa Maria FernándezBiochemistry and Molecular Genetics Department, Biomedical Diagnostic Center, Hospital Clínic, Villarroel 170, 08036 Barcelona, Spain.ORCID 0000-0001-5873-4961
Judit García-VilloriaAdult Inborn Errors of Metabolism Unit, Hospital Clínic, Villarroel 170, 08036 Barcelona, Spain.ORCID 0000-0003-2132-4138
Glòria GarrabouAdult Inborn Errors of Metabolism Unit, Hospital Clínic, Villarroel 170, 08036 Barcelona, Spain.ORCID 0000-0001-8973-9933
Irene VinagreEndocrinology and Nutrition Department, Hospital Clínic, Villarroel 170, 08036 Barcelona, Spain.
Laura M TannerFetomaternal Medical Center and Department of Clinical Genetics, Helsinki University Hospital, Department of Medical and Clinical Genetics, University of Helsinki, 00251 Helsinki, Finland.
Cristina Montserrat-CarbonellEndocrinology and Nutrition Department, Hospital Clínic, Villarroel 170, 08036 Barcelona, Spain.ORCID 0009-0009-3917-0334
Maria de Talló Forga-VisaEndocrinology and Nutrition Department, Hospital Clínic, Villarroel 170, 08036 Barcelona, Spain.
Hospital Clínic de Barcelona · ESInstituto de Salud Carlos III · ESUniversity of Helsinki · FI

Funding

No grant is acknowledged in the PubMed record.

6 · The paper itself

Abstract

Lysinuric protein intolerance (LPI) is a rare inborn error of metabolism (IEM), classified as an inherited aminoaciduria, caused by mutations in the SLC7A7 gene, leading to a defective cationic amino acid transport. The metabolic adaptations to the demands of pregnancy and delivery cause significant physiological stress, so those patients affected by IEM are at greater risk of decompensation. A 28-year-old woman with LPI had experienced 3 early miscarriages. While pregnancy was finally achieved, diverse nutritional and medical challenges emerged (food aversion, intrauterine growth restriction, bleeding risk, and preeclampsia suspicion), which put both the mother and the fetus at risk. Moreover, the patient requested a natural childbirth (epidural-free, delayed cord clamping). Although the existence of multiple safety concerns rejected this approach at first, the application of novel strategies made a successful delivery possible. This case reinforces that the woman's wish for a non-medicated, low-intervention natural birth should not be automatically discouraged because of an underlying complex metabolic condition. Achieving a successful pregnancy is conceivable thanks to the cooperation of interdisciplinary teams, but it is still important to consider the risks beforehand in order to be prepared for possible additional complications.

Indexed as

hyperammonemiainborn error of metabolismlysinuric protein intolerancenutritionpregnancyrare disease

Identifiers

PMID37835050
PMCPMC10573933
OpenAlexW4387455061

What OpenQuestion holds

Textmetadata
LicenceCC BY
Read underepoch 390

Registered trials

None linked

Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the OpenQuestion graph.