Evidence map›Paper›PMID 37768187›Full record

ArticleAmerican journal of medical genetics. Part A2024

Parental age effects and Rett syndrome.

Xiaolan Fang, Lauren M Baggett, Raymond C Caylor, Alan K Percy, Jeffrey L Neul, Jane B Lane, Daniel G Glaze, Tim A Benke, Eric D Marsh, Kathleen J Motil and 3 more

Open access · greenAbstract read
In one paragraph

Article in American journal of medical genetics. Part A, 2024. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Cited by 3 papers.

0numbers the graph read from it
0cells of the map it votes in
3citing papers in PubMed
0.9field-weighted citation impact, top 19% of its field
1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

Trials whose registry record cites this paper, or whose number appears in the abstract. A trial that started after this paper was published is citing it as background, not reporting it.

Neither the registry nor the abstract names a trial number. If this is a trial report, that itself is worth knowing.

3 · Its place in the literature

Who cites it

3 citing papers in PubMed, 3 citations in OpenAlex.

  1. Review
  2. Review
  3. Rett syndrome: The Natural History Study journey.Annals of the Child Neurology Society · 2024
    Review
4 · The record

Corrections and comments

PubMed lists nothing against this paper. Absence here is not a guarantee, only a check that was made.

5 · Who and what money

Authors and funding

13 authors at 6 institutions in 1 country.

Xiaolan FangGreenwood Genetic Center, Greenwood, South Carolina, USA.ORCID 0000-0002-7056-7585
Lauren M BaggettGreenwood Genetic Center, Greenwood, South Carolina, USA.
Raymond C CaylorGreenwood Genetic Center, Greenwood, South Carolina, USA.ORCID 0000-0003-1067-2807
Alan K PercyThe University of Alabama at Birmingham, Birmingham, Alabama, USA.
Jeffrey L NeulVanderbilt Kennedy Center, Vanderbilt University Medical Center, Nashville, Tennessee, USA.ORCID 0000-0002-5628-5872
Jane B LaneThe University of Alabama at Birmingham, Birmingham, Alabama, USA.
Daniel G GlazeBaylor College of Medicine, Houston, Texas, USA.
Tim A BenkeUniversity of Colorado School of Medicine, Children's Hospital Colorado-Aurora, Denver, Colorado, USA.ORCID 0000-0002-6969-5061
Eric D MarshChildren's Hospital of Philadelphia and University of Pennsylvania, Philadelphia, Pennsylvania, USA.ORCID 0000-0003-3264-0902
Kathleen J MotilVanderbilt Kennedy Center, Vanderbilt University Medical Center, Nashville, Tennessee, USA.
Judy O BarrishBaylor College of Medicine, Houston, Texas, USA.
Fran E AnneseGreenwood Genetic Center, Greenwood, South Carolina, USA.
Steven A SkinnerGreenwood Genetic Center, Greenwood, South Carolina, USA.ORCID 0000-0003-3844-0792
Greenwood Genetic Center · USBaylor College of Medicine · USUniversity of Alabama at Birmingham · USVanderbilt University Medical Center · USChildren's Hospital Colorado · USChildren's Hospital of Philadelphia · US

Funding

Training and Career Development ComponentU54HD061222 · NICHD · UNIVERSITY OF ALABAMA AT BIRMINGHAM · PI PERCY, ALAN KENNETH · 2009 to 2019
$12.4M
Overall: Eunice Kennedy Shriver Intellectual and Developmental Disabilities Research Center at VanderbiltP50HD103537 · NICHD · VANDERBILT UNIVERSITY MEDICAL CENTER · PI Jeffrey L Neul · 2020 to 2026
$10.3M
NCATS NIH HHSNICHD NIH HHS P50 HD103537NICHD NIH HHS U54 HD061222NIH HHS
6 · The paper itself

Abstract

Rett syndrome (RTT) is a progressive neurodevelopmental disorder, and pathogenic Methyl-CpG-binding Protein 2 (MECP2) variants are identified in >95% of individuals with typical RTT. Most of RTT-causing variants in MECP2 are de novo and usually on the paternally inherited X chromosome. While paternal age has been reported to be associated with increased risk of genetic disorders, it is unknown whether parental age contributes to the risk of the development of RTT. Clinical data including parental age, RTT diagnostic status, and clinical severity are collected from 1226 participants with RTT and confirmed MECP2 variants. Statistical analyses are performed using Student t-test, single factor analysis of variance (ANOVA), and multi-factor regression. No significant difference is observed in parental ages of RTT probands compared to that of the general population. A small increase in parental ages is observed in participants with missense variants compared to those with nonsense variants. When we evaluate the association between clinical severity and parental ages by multiple regression analysis, there is no clear association between clinical severity and parental ages. Advanced parental ages do not appear to be a risk factor for RTT, and do not contribute to the clinical severity in individuals with RTT.

Indexed as

Rett SyndromeChromosomes, Human, XHumansMethyl-CpG-Binding Protein 2MutationParentsMethyl-CpG-Binding Protein 2clinical severityMECP2parental ageRETT syndromerisk factor

Identifiers

PMID37768187
PMCPMC11911005
OpenAlexW4387116145

What OpenQuestion holds

Textmetadata
LicenceTDM
Read underepoch 390

Registered trials

None linked

Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the OpenQuestion graph.