Evidence map›Paper›PMID 37672513›Full record

ArticlePloS one2023

Identification of candidate genes for developmental colour agnosia in a single unique family.

Tanja C W Nijboer, Ellen V S Hessel, Gijs W van Haaften, Martine J van Zandvoort, Peter J van der Spek, Christine Troelstra, Carolien G F de Kovel, Bobby P C Koeleman, Bert van der Zwaag, Eva H Brilstra and 1 more

Open access · goldAbstract read
In one paragraph

Article in PloS one, 2023. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Cited by 1 paper.

0numbers the graph read from it
0cells of the map it votes in
1citing papers in PubMed
–field-weighted citation impact, top 84% of its field
1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

Trials whose registry record cites this paper, or whose number appears in the abstract. A trial that started after this paper was published is citing it as background, not reporting it.

Neither the registry nor the abstract names a trial number. If this is a trial report, that itself is worth knowing.

3 · Its place in the literature

Who cites it

1 citing paper in PubMed, 0 citations in OpenAlex.

  1. Article
4 · The record

Corrections and comments

PubMed lists nothing against this paper. Absence here is not a guarantee, only a check that was made.

5 · Who and what money

Authors and funding

11 authors at 3 institutions in 1 country.

Tanja C W NijboerUMCU Brain Center and Center of Excellence for Rehabilitation Medicine, University Medical Center Utrecht and De Hoogstraat Rehabilitation, Utrecht, The Netherlands.ORCID 0000-0001-6683-0267
Ellen V S HesselUMCU Brain Center and Center of Excellence for Rehabilitation Medicine, University Medical Center Utrecht and De Hoogstraat Rehabilitation, Utrecht, The Netherlands.
Gijs W van HaaftenDepartment of Biomedical Genetics, University Medical Center Utrecht, Utrecht, The Netherlands.
Martine J van ZandvoortDepartment of Experimental Psychology and Helmholtz Institute, Utrecht University, Utrecht, The Netherlands.
Peter J van der SpekDepartment of Pathology, Erasmus Medical Center Rotterdam, Rotterdam, the Netherlands.
Christine TroelstraDepartment of Pathology, Erasmus Medical Center Rotterdam, Rotterdam, the Netherlands.
Carolien G F de KovelDepartment of Biomedical Genetics, University Medical Center Utrecht, Utrecht, The Netherlands.ORCID 0000-0002-7818-1396
Bobby P C KoelemanDepartment of Biomedical Genetics, University Medical Center Utrecht, Utrecht, The Netherlands.
Bert van der ZwaagDepartment of Biomedical Genetics, University Medical Center Utrecht, Utrecht, The Netherlands.
Eva H BrilstraDepartment of Biomedical Genetics, University Medical Center Utrecht, Utrecht, The Netherlands.
J Peter H BurbachUMCU Brain Center, Department of Translational Neuroscience, University Medical Center Utrecht, Utrecht, the Netherlands.ORCID 0000-0002-8619-6168
University Medical Center Utrecht · NLErasmus MC · NLUtrecht University · NL

Funding

No grant is acknowledged in the PubMed record.

6 · The paper itself

Abstract

Colour agnosia is a disorder that impairs colour knowledge (naming, recognition) despite intact colour perception. Previously, we have identified the first and only-known family with hereditary developmental colour agnosia. The aim of the current study was to explore genomic regions and candidate genes that potentially cause this trait in this family. For three family members with developmental colour agnosia and three unaffected family members CGH-array analysis and exome sequencing was performed, and linkage analysis was carried out using DominantMapper, resulting in the identification of 19 cosegregating chromosomal regions. Whole exome sequencing resulted in 11 rare coding variants present in all affected family members with developmental colour agnosia and absent in unaffected members. These variants affected genes that have been implicated in neural processes and functions (CACNA2D4, DDX25, GRINA, MYO15A) or that have an indirect link to brain function, development or disease (MAML2, STAU1, TMED3, RABEPK), and a remaining group lacking brain expression or involved in non-neural traits (DEPDC7, OR1J1, OR8D4). Although this is an explorative study, the small set of candidate genes that could serve as a starting point for unravelling mechanisms of higher level cognitive functions and cortical specialization, and disorders therein such as developmental colour agnosia.

Indexed as

AgnosiaBrainColorCytoskeletal ProteinsHumansRNA-Binding ProteinsVesicular Transport ProteinsCytoskeletal ProteinsRNA-Binding ProteinsSTAU1 protein, humanTMED3 protein, humanVesicular Transport Proteins

Identifiers

PMID37672513
PMCPMC10482254
OpenAlexW4386470235

What OpenQuestion holds

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LicenceCC BY
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Registered trials

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Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the OpenQuestion graph.