Evidence map›Paper›PMID 36430820›Full record

ArticleInternational journal of molecular sciences2022

Targeted NGS in Diagnostics of Genodermatosis Characterized by the Epidermolysis Bullosa Symptom Complex in 268 Russian Children.

Kirill Savostyanov, Nikolay Murashkin, Alexander Pushkov, Ilya Zhanin, Elkhan Suleymanov, Mariya Akhkiamova, Olga Shchagina, Elena Balanovska, Roman Epishev, Aleksander Polyakov and 1 more

Open access · goldAbstract read
In one paragraph

Article in International journal of molecular sciences, 2022. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Cited by 4 papers.

0numbers the graph read from it
0cells of the map it votes in
4citing papers in PubMed
0.6field-weighted citation impact, top 38% of its field
1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

Trials whose registry record cites this paper, or whose number appears in the abstract. A trial that started after this paper was published is citing it as background, not reporting it.

Neither the registry nor the abstract names a trial number. If this is a trial report, that itself is worth knowing.

3 · Its place in the literature

Who cites it

4 citing papers in PubMed, 5 citations in OpenAlex.

  1. Article
  2. Article
  3. Review
  4. Review
4 · The record

Corrections and comments

PubMed lists nothing against this paper. Absence here is not a guarantee, only a check that was made.

5 · Who and what money

Authors and funding

11 authors at 2 institutions in 1 country.

Kirill SavostyanovFSAI «National Medical Research Center for Children's Health» of the Russian Federation Ministry of Health, 119991 Moscow, Russia.ORCID 0000-0003-4885-4171
Nikolay MurashkinFSAI «National Medical Research Center for Children's Health» of the Russian Federation Ministry of Health, 119991 Moscow, Russia.
Alexander PushkovFSAI «National Medical Research Center for Children's Health» of the Russian Federation Ministry of Health, 119991 Moscow, Russia.
Ilya ZhaninFSAI «National Medical Research Center for Children's Health» of the Russian Federation Ministry of Health, 119991 Moscow, Russia.ORCID 0000-0003-1423-0379
Elkhan SuleymanovMinistry of Public Health, Republic of Chechnya, 364037 Grozny, Russia.
Mariya AkhkiamovaResearch Centre for Medical Genetics, 115522 Moscow, Russia.
Olga ShchaginaResearch Centre for Medical Genetics, 115522 Moscow, Russia.ORCID 0000-0003-4905-1303
Elena BalanovskaResearch Centre for Medical Genetics, 115522 Moscow, Russia.
Roman EpishevFSAI «National Medical Research Center for Children's Health» of the Russian Federation Ministry of Health, 119991 Moscow, Russia.
Aleksander PolyakovResearch Centre for Medical Genetics, 115522 Moscow, Russia.
Andrey FisenkoFSAI «National Medical Research Center for Children's Health» of the Russian Federation Ministry of Health, 119991 Moscow, Russia.
Ministry of Health of the Russian Federation · RUResearch Centre for Medical Genetics · RU

Funding

Ministry of Science and Higher Education of the Russian Federation 0520-2019-0029
6 · The paper itself

Abstract

The pathogenic variants of genes encoding proteins, participating in the formation and functioning of epidermis and dermo-epidermal junctions, create a large variety of clinical phenotypes from: small localized to severe generalized dermatitis, as well as early, or even, prenatal death due to extensive epidermis loss. The diagnostic panel in this study was developed for the purposes of identifying these pathogenic genetic variants in 268 Russian children, who possessed the epidermolysis bullosa symptom complex in a selection of 247 families. This panel included the targeted areas of 33 genes, which are genetic variants that can lead to the development of the phenotype mentioned above. The usage of next generation sequencing allowed the revelation of 192 various altered alleles (of which 109 alleles were novel, i.e., had not been described previously). In addition, it allowed the definition of the genetic variants that are both typical for most of the examined children and for the separate ethnic groups inhabiting modern Russia. We found that the most characteristic mutations for the Dargin and Chechen ethnic groups are the c.3577del deletion in the COL7A1 gene and the c.2488G>A missense mutation in the COL17A1 gene, respectively. In addition, the study of haplotypes of microsatellite markers, which we managed to conduct in the Dargin population, confirmed the presence of the founder effect.

Indexed as

Epidermolysis BullosaAllelesCollagen Type VIIHigh-Throughput Nucleotide SequencingHumansMutationPhenotypeCOL7A1 protein, humanCollagen Type VIIchildrenepidermolysis bullosafounder effectmicrosatellite markersnext generation sequencing

Identifiers

PMID36430820
PMCPMC9698894
OpenAlexW4309744084

What OpenQuestion holds

Textmetadata
LicenceCC BY
Read underepoch 390

Registered trials

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Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the OpenQuestion graph.