Evidence map›Paper›PMID 36267859›Full record

ArticleJournal of pediatric genetics2022

A Case Report: Two Young Children with Long QT Syndrome Type-2 Diagnosed by Presymptomatic Genetic Testing.

Yuki Matsushita, Hazumu Nagata, Masanobu Ogawa, Sawako Shikada, Taisuke Ishikawa, Naomasa Makita

Open access · greenAbstract readCase Reports
In one paragraph

Article in Journal of pediatric genetics, 2022. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Cited by 2 papers.

0numbers the graph read from it
0cells of the map it votes in
2citing papers in PubMed
–field-weighted citation impact, top 73% of its field
1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

Trials whose registry record cites this paper, or whose number appears in the abstract. A trial that started after this paper was published is citing it as background, not reporting it.

Neither the registry nor the abstract names a trial number. If this is a trial report, that itself is worth knowing.

3 · Its place in the literature

Who cites it

2 citing papers in PubMed, 2 citations in OpenAlex.

  1. Article
  2. Article
4 · The record

Corrections and comments

PubMed lists nothing against this paper. Absence here is not a guarantee, only a check that was made.

5 · Who and what money

Authors and funding

6 authors at 4 institutions in 1 country.

Yuki MatsushitaDepartment of Pediatrics, Clinical Research Institute, National Hospital Organization, Kyushu Medical Center, Fukuoka, Japan.ORCID 0000-0002-8276-8616
Hazumu NagataDepartment of Pediatrics, Graduate School of Medical Sciences, Kyushu University, Fukuoka, Japan.
Masanobu OgawaResearch Center for Environmental and Developmental Medical Sciences, Kyushu University, Fukuoka, Japan.ORCID 0000-0002-4559-1997
Sawako ShikadaDepartment of Clinical Genetics and Medicine, Kyushu University Hospital, Fukuoka, Japan.
Taisuke IshikawaOmics Research Center, National Cerebral and Cardiovascular Center, Suita, Japan.ORCID 0000-0001-8195-4700
Naomasa MakitaOmics Research Center, National Cerebral and Cardiovascular Center, Suita, Japan.ORCID 0000-0002-1807-672X
Kyushu University · JPNational Cerebral and Cardiovascular Center · JPKyushu University Hospital · JPNational Kyushu Medical Center · JP

Funding

No grant is acknowledged in the PubMed record.

6 · The paper itself

Abstract

Long QT syndromes (LQTSs) can lead to sudden cardiac death, yet these syndromes are often asymptomatic and clinically undetected, despite the prolongation of the QT interval. Currently, when a disease-causing variant is identified in an individual, presymptomatic genetic testing is available and can form part of the recommended cascade testing to identify other family members at risk. We herein report the cases of two daughters who received presymptomatic genetic testing in infancy when the proband mother had been diagnosed with LQTS type 2 (LQT2; c.1171C > T, p.Q391X in KCNH2) after suffering from cardiac arrhythmia at 30 years of age. The daughters had a normal QTc interval, but they carried the same disease-causing variant as their mother. Children with family members who have genetically confirmed LQTS have a high risk of suffering from cardiac events later in life, so genetic testing is required. This poses a complex problem, as guidelines for medical intervention and follow-up systems among asymptomatic children with LQTS have yet to be established. Genetic testing should only be performed after adequate counseling to support children later in life. Individualized long-term genetic counseling is required for both parents and children at stages throughout life.

Indexed as

genetic counselinglong QT syndromepathogenic variantpresymptomatic genetic testing

Identifiers

PMID36267859
PMCPMC9578781
OpenAlexW3109738246

What OpenQuestion holds

Textmetadata
Read underepoch 390

Registered trials

None linked

Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the OpenQuestion graph.