Evidence map›Paper›PMID 34973099›Full record

ArticleAnnals of hematology2022

The burden of illness in patients with paroxysmal nocturnal hemoglobinuria receiving treatment with the C5-inhibitors eculizumab or ravulizumab: results from a US patient survey.

David Dingli, Joana E Matos, Kerri Lehrhaupt, Sangeeta Krishnan, Michael Yeh, Jesse Fishman, Sujata P Sarda, Scott B Baver

Open access · hybridAbstract read
In one paragraph

Article in Annals of hematology, 2022. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Cited by 45 papers, 2 of them syntheses that pooled it.

0numbers the graph read from it
0cells of the map it votes in
45citing papers in PubMed, 2 pooled it
4.4field-weighted citation impact, top 4% of its field
1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

Trials whose registry record cites this paper, or whose number appears in the abstract. A trial that started after this paper was published is citing it as background, not reporting it.

Neither the registry nor the abstract names a trial number. If this is a trial report, that itself is worth knowing.

3 · Its place in the literature

Who cites it

45 citing papers in PubMed, 2 syntheses or guidelines pooled it, 55 citations in OpenAlex.

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4 · The record

Corrections and comments

PubMed lists nothing against this paper. Absence here is not a guarantee, only a check that was made.

5 · Who and what money

Authors and funding

8 authors at 3 institutions in 1 country.

David DingliMayo Clinic, Rochester, MN, USA. dingli.david@mayo.edu.ORCID http://orcid.org/0000-0001-7477-3004
Joana E MatosKantar Health, New York, NY, USA.
Kerri LehrhauptKantar Health, New York, NY, USA.
Sangeeta KrishnanApellis Pharmaceuticals, Inc., Waltham, MA, USA.
Michael YehApellis Pharmaceuticals, Inc., Waltham, MA, USA.
Jesse FishmanApellis Pharmaceuticals, Inc., Waltham, MA, USA.
Sujata P SardaApellis Pharmaceuticals, Inc., Waltham, MA, USA.
Scott B BaverApellis Pharmaceuticals, Inc., Waltham, MA, USA.
Apellis Pharmaceuticals (United States) · USKantar Health (United States) · USMayo Clinic in Arizona · US

Funding

No grant is acknowledged in the PubMed record.

6 · The paper itself

Abstract

Paroxysmal nocturnal hemoglobinuria (PNH) is a rare and life-threatening disease with symptoms of hemolysis and thrombosis. Current therapies for this complement-mediated disease rely predominantly on inhibition of the C5 complement protein. However, data on treatment responses and quality of life in C5-inhibitor (C5i)-treated PNH patients are scarce. The objective of this study was to determine C5i treatment effects on clinical parameters, PNH symptoms, quality of life, and resource use for PNH patients. This cross-sectional study surveyed 122 individuals in the USA receiving treatment for PNH with C5-targeted monoclonal antibodies, eculizumab (ECU) or ravulizumab (RAV). Despite most patients receiving C5i therapy for ≥ 3 months (ECU 100%, n = 35; RAV 95.4%, n = 83), many patients remained anemic with hemoglobin levels ≤ 12 g/dL in 87.5% (n = 28/32) and 82.9% (n = 68/82) of ECU and RAV recipients, respectively. A majority of patients on ECU (88.6%; n = 31/35) and RAV (74.7%; n = 65/87) reported fatigue symptoms. Among PNH patients receiving C5i therapy for ≥ 12 months, some still reported thrombotic events (ECU, 10.0%, n = 1/10; RAV, 23.5%, n = 4/17) and required transfusions within the past year (ECU, 52.2%, n = 12/23; RAV, 22.6%, n = 7/31). Other patient-reported PNH symptoms included breakthrough hemolysis, shortness of breath, and headaches. Patients reported scores below the average population norms on the Functional Assessment of Chronic Illness Therapy (FACIT)-Fatigue and European Organization for Research and Treatment of Cancer Quality of Life Questionnaire Core 30 (EORTC QLQ-C30) scales. Overall, this study found that PNH patients receiving ECU or RAV therapy demonstrated a significant burden of illness, highlighting the need for improved PNH therapies.

Indexed as

AdultAgedAntibodies, Monoclonal, HumanizedComplement Inactivating AgentsCost of IllnessCross-Sectional StudiesFemaleHemoglobinuria, ParoxysmalHumansMaleMiddle AgedQuality of LifeSurveys and QuestionnairesUnited StatesAntibodies, Monoclonal, HumanizedComplement Inactivating AgentseculizumabravulizumabBurden of illnessEculizumabFatigueParoxysmal nocturnal hemoglobinuriaQuality of lifeRavulizumab

Identifiers

PMID34973099
PMCPMC8720163
OpenAlexW4206061362

What OpenQuestion holds

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LicenceCC BY
Read underepoch 390

Registered trials

None linked

Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the OpenQuestion graph.