Evidence map›Paper›PMID 34802434›Full record

ArticleJournal of cardiothoracic surgery2021

Neonatal repair of total anomalous pulmonary venous connection accompanied by unilateral lung agenesis and Goldenhar syndrome: a case report.

Takahiro Ito, Ikuo Hagino, Mitsuru Aoki, Kentaro Umezu, Tomohiro Saito, Akiyo Suzuki

Open access · goldAbstract readCase Reports
In one paragraph

Article in Journal of cardiothoracic surgery, 2021. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Cited by 3 papers.

0numbers the graph read from it
0cells of the map it votes in
3citing papers in PubMed
–field-weighted citation impact, top 74% of its field
1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

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3 · Its place in the literature

Who cites it

3 citing papers in PubMed, 3 citations in OpenAlex.

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4 · The record

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5 · Who and what money

Authors and funding

6 authors at 1 institution in 1 country.

Takahiro ItoDepartment of Cardiovascular Surgrey, Chiba Children's Hospital, 579-1 Heta, Midori, Chiba-city, Chiba, 266-0007, Japan.ORCID http://orcid.org/0000-0003-2101-2732
Ikuo HaginoDepartment of Cardiovascular Surgrey, Chiba Children's Hospital, 579-1 Heta, Midori, Chiba-city, Chiba, 266-0007, Japan. ihagino@e23.jp.
Mitsuru AokiDepartment of Cardiovascular Surgrey, Chiba Children's Hospital, 579-1 Heta, Midori, Chiba-city, Chiba, 266-0007, Japan.
Kentaro UmezuDepartment of Cardiovascular Surgrey, Chiba Children's Hospital, 579-1 Heta, Midori, Chiba-city, Chiba, 266-0007, Japan.
Tomohiro SaitoDepartment of Cardiovascular Surgrey, Chiba Children's Hospital, 579-1 Heta, Midori, Chiba-city, Chiba, 266-0007, Japan.
Akiyo SuzukiDepartment of Cardiovascular Surgrey, Chiba Children's Hospital, 579-1 Heta, Midori, Chiba-city, Chiba, 266-0007, Japan.
Chiba Hospital · JP

Funding

No grant is acknowledged in the PubMed record.

6 · The paper itself

Abstract

backgroundTotal anomalous pulmonary venous connection accompanied by unilateral lung agenesis and Goldenhar syndrome is extremely rare. CASE PRESENTATION: We present a case of total anomalous pulmonary venous connection accompanied by unilateral lung agenesis and Goldenhar syndrome in a patient who was diagnosed based on transthoracic echocardiography and computed tomography. We observed complete absence of the lung, the bronchial tree, and vascular structures on the right side, with abnormal drainage of the left pulmonary veins into the innominate vein. The patient showed clear clinical evidence of pulmonary venous obstruction and underwent surgery 3 days after birth. The pulmonary venous chamber containing the vertical vein was anastomosed to the left atrium using 7-0 PDS running sutures via a median sternotomy. Echocardiography and computed tomography performed 1 year postoperatively revealed no pulmonary venous obstruction.

conclusionWe report a rare case of total anomalous pulmonary venous connection accompanied by unilateral lung agenesis and Goldenhar syndrome, which was successfully repaired 3 days after birth. A median sternotomy is a safe and effective approach for surgical repair of congenital heart disease with unilateral lung agenesis. Repair of the supra cardiac total anomalous pulmonary connection using the vertical vein is feasible in patients with a small pulmonary venous chamber.

Indexed as

Goldenhar SyndromeLung DiseasesPulmonary VeinsAbnormalities, MultipleHeart AtriaHumansInfant, NewbornLungGoldenhar syndromeTotal anomalous pulmonary venous connectionUnilateral lung agenesis

Identifiers

PMID34802434
PMCPMC8607644
OpenAlexW3217752375

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Registered trials

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Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the OpenQuestion graph.