Evidence map›Paper›PMID 33498938›Full record

ArticleBiomolecules2021

Prepubertal Periodontitis in a Patient with Combined Classical and Periodontal Ehlers-Danlos Syndrome.

Friedrich Stock, Marcel Hanisch, Sarah Lechner, Saskia Biskup, Axel Bohring, Johannes Zschocke, Ines Kapferer-Seebacher

Open access · goldAbstract readCase Reports
In one paragraph

Article in Biomolecules, 2021. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Cited by 5 papers.

0numbers the graph read from it
0cells of the map it votes in
5citing papers in PubMed
1.4field-weighted citation impact, top 18% of its field
1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

Trials whose registry record cites this paper, or whose number appears in the abstract. A trial that started after this paper was published is citing it as background, not reporting it.

Neither the registry nor the abstract names a trial number. If this is a trial report, that itself is worth knowing.

3 · Its place in the literature

Who cites it

5 citing papers in PubMed, 10 citations in OpenAlex.

  1. Review
  2. Article
  3. Article
  4. Oral manifestations of Ehlers-Danlos syndromes.American journal of medical genetics. Part C, Seminars in medical genetics · 2021
    Review
  5. Article
4 · The record

Corrections and comments

PubMed lists nothing against this paper. Absence here is not a guarantee, only a check that was made.

5 · Who and what money

Authors and funding

7 authors at 3 institutions in 2 countries.

Friedrich StockInstitute of Human Genetics, University Hospital Münster, Vesaliusweg 12, D-48149 Münster, Germany.
Marcel HanischResearch Unit Rare Diseases with Orofacial, Manifestations (RDOM), Department of Cranio-Maxillofacial Surgery, University Hospital Münster, Albert-Schweitzer-Campus 1, Building W 30, D-48149 Münster, Germany.
Sarah LechnerPraxis für Humangenetik Tübingen, Paul-Ehrlich-Straße 23, D-72076 Tübingen, Germany.
Saskia BiskupPraxis für Humangenetik Tübingen, Paul-Ehrlich-Straße 23, D-72076 Tübingen, Germany.
Axel BohringInstitute of Human Genetics, University Hospital Münster, Vesaliusweg 12, D-48149 Münster, Germany.
Johannes ZschockeInstitute of Human Genetics, Medical University of Innsbruck, Peter-Mayr-Straße 1, A-6020 Innsbruck, Austria.ORCID 0000-0002-0046-8274
Ines Kapferer-SeebacherDepartment of Operative and Restorative Dentistry, Medical University of Innsbruck, Anichstraße 35, A-6020 Innsbruck, Austria.ORCID 0000-0001-6169-6812
University Hospital Münster · DEInnsbruck Medical University · ATPraxis für Humangenetik Tübingen · DE

Funding

No grant is acknowledged in the PubMed record.

6 · The paper itself

Abstract

We report an extremely rare case of combined classical and periodontal Ehlers-Danlos syndrome (EDS) with early severe periodontitis and a generalized lack of attached gingiva. A German family with classical EDS was investigated by physical and dental evaluation and exome and Sanger sequencing. Due to the specific periodontal phenotype in the affected child, an additional diagnosis of periodontal EDS was suspected. Physical and genetic examination of two affected and three unaffected family members revealed a family diagnosis of classical EDS with a heterozygous mutation in COL5A1 (c.1502del; p.Pro501Leufs*57). Additional to the major clinical criteria for classical EDS-generalized joint hypermobility, hyperelastic skin, and atrophic scarring -the child aged four years presented with generalized alveolar bone loss up to 80%, early loss of two lower incisors, severe gingival recession, and generalized lack of attached gingiva. Due to these clinical findings, an additional diagnosis of periodontal EDS was suspected. Further genetic analysis revealed the novel missense mutation c.658T>G (p.Cys220Gly) in C1R in a heterozygous state. Early severe periodontitis in association with generalized lack of attached gingiva is pathognomonic for periodontal EDS and led to the right clinical and genetic diagnosis in the present case.

Indexed as

Child, PreschoolCollagen Type VComplement C1rEhlers-Danlos SyndromeExomeFamily HealthFemaleHeterozygoteHumansInflammationMutationPeriodontal DiseasesPhenotypeSequence Analysis, DNACOL5A1 protein, humanCollagen Type VComplement C1rC1RcomplementEhlers−Danlos syndromeperiodontitistype V collagen

Identifiers

PMID33498938
PMCPMC7912441
OpenAlexW3123280784

What OpenQuestion holds

Textmetadata
LicenceCC BY
Read underepoch 390

Registered trials

None linked

Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the OpenQuestion graph.