Evidence map›Paper›PMID 31920494›Full record

ArticleFrontiers in neuroscience2019

A Targeted Gene Panel That Covers Coding, Non-coding and Short Tandem Repeat Regions Improves the Diagnosis of Patients With Neurodegenerative Diseases.

Allen Chi-Shing Yu, Aldrin Kay-Yuen Yim, Anne Yin-Yan Chan, Liz Y P Yuen, Wing Chi Au, Timothy H T Cheng, Xiao Lin, Jing-Woei Li, Larry W L Chan, Vincent C T Mok and 2 more

Open access · goldAbstract read
In one paragraph

Article in Frontiers in neuroscience, 2019. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Cited by 7 papers.

0numbers the graph read from it
0cells of the map it votes in
7citing papers in PubMed
0.4field-weighted citation impact, top 42% of its field
1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

Trials whose registry record cites this paper, or whose number appears in the abstract. A trial that started after this paper was published is citing it as background, not reporting it.

Neither the registry nor the abstract names a trial number. If this is a trial report, that itself is worth knowing.

3 · Its place in the literature

Who cites it

7 citing papers in PubMed, 10 citations in OpenAlex.

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  5. Review
  6. Genetic Inheritance and Its Contribution to Tinnitus.Current topics in behavioral neurosciences · 2021
    Review
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4 · The record

Corrections and comments

PubMed lists nothing against this paper. Absence here is not a guarantee, only a check that was made.

5 · Who and what money

Authors and funding

12 authors at 3 institutions in 2 countries.

Allen Chi-Shing YuCodex Genetics Limited, Shatin, Hong Kong.
Aldrin Kay-Yuen YimCodex Genetics Limited, Shatin, Hong Kong.
Anne Yin-Yan ChanDivision of Neurology, Department of Medicine and Therapeutics, The Chinese University of Hong Kong, Shatin, China.
Liz Y P YuenDepartment of Chemical Pathology, The Chinese University of Hong Kong, Shatin, China.
Wing Chi AuDivision of Neurology, Department of Medicine and Therapeutics, The Chinese University of Hong Kong, Shatin, China.
Timothy H T ChengDepartment of Chemical Pathology, The Chinese University of Hong Kong, Shatin, China.
Xiao LinSchool of Life Sciences, The Chinese University of Hong Kong, Shatin, China.
Jing-Woei LiCodex Genetics Limited, Shatin, Hong Kong.
Larry W L ChanAlice Ho Miu Ling Nethersole Hospital, Tai Po, Hong Kong.
Vincent C T MokDivision of Neurology, Department of Medicine and Therapeutics, The Chinese University of Hong Kong, Shatin, China.
Ting-Fung ChanCodex Genetics Limited, Shatin, Hong Kong.
Ho Yin Edwin ChanCodex Genetics Limited, Shatin, Hong Kong.
Chinese University of Hong Kong · CNAlice Ho Miu Ling Nethersole Hospital · CNWashington University in St. Louis · US

Funding

No grant is acknowledged in the PubMed record.

6 · The paper itself

Abstract

Genetic testing for neurodegenerative diseases (NDs) is highly challenging because of genetic heterogeneity and overlapping manifestations. Targeted-gene panels (TGPs), coupled with next-generation sequencing (NGS), can facilitate the profiling of a large repertoire of ND-related genes. Due to the technical limitations inherent in NGS and TGPs, short tandem repeat (STR) variations are often ignored. However, STR expansions are known to cause such NDs as Huntington's disease and spinocerebellar ataxias type 3 (SCA3). Here, we studied the clinical utility of a custom-made TGP that targets 199 NDs and 311 ND-associated genes on 118 undiagnosed patients. At least one known or likely pathogenic variation was found in 54 patients; 27 patients demonstrated clinical profiles that matched the variants; and 16 patients whose original diagnosis were refined. A high concordance of variant calling were observed when comparing the results from TGP and whole-exome sequencing of four patients. Our in-house STR detection algorithm has reached a specificity of 0.88 and a sensitivity of 0.82 in our SCA3 cohort. This study also uncovered a trove of novel and recurrent variants that may enrich the repertoire of ND-related genetic markers. We propose that a combined comprehensive TGPs-bioinformatics pipeline can improve the clinical diagnosis of NDs.

Indexed as

clinical decision supportgene panelhigh-throughput sequencingneurodegenerative diseasesshort tandem repeatundiagnosed diseases

Identifiers

PMID31920494
PMCPMC6917647
OpenAlexW2990160845

What OpenQuestion holds

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Registered trials

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Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the OpenQuestion graph.