Evidence map›Paper›PMID 31758390›Full record

ArticleGeneral thoracic and cardiovascular surgery2020

Alport-leiomyomatosis syndrome requiring subtotal esophagectomy for refractory gastroesophageal reflux disease after childhood partial esophagogastrectomy: a case report.

Junya Aoyama, Yutaka Miyawaki, Takuya Kato, Naoto Fujiwara, Hirofumi Sugita, Hiroshi Sato, Masanori Yasuda, Shinichi Sakuramoto, Shigeki Yamaguchi

Abstract readCase Reports
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In one paragraph

Article in General thoracic and cardiovascular surgery, 2020. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Cited by 2 papers.

0numbers the graph read from it
0cells of the map it votes in
2citing papers in PubMed
0.3field-weighted citation impact, top 36% of its field
1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

Trials whose registry record cites this paper, or whose number appears in the abstract. A trial that started after this paper was published is citing it as background, not reporting it.

Neither the registry nor the abstract names a trial number. If this is a trial report, that itself is worth knowing.

3 · Its place in the literature

Who cites it

2 citing papers in PubMed, 4 citations in OpenAlex.

  1. Review
  2. Article
4 · The record

Corrections and comments

PubMed lists nothing against this paper. Absence here is not a guarantee, only a check that was made.

5 · Who and what money

Authors and funding

9 authors at 1 institution in 1 country.

Junya AoyamaDepartment of Gastroenterological Surgery, Saitama Medical University International Medical Center, Hidaka, Japan.
Yutaka MiyawakiDepartment of Gastroenterological Surgery, Saitama Medical University International Medical Center, Hidaka, Japan. miysrg1@tmd.ac.jp.
Takuya KatoDepartment of Gastroenterological Surgery, Saitama Medical University International Medical Center, Hidaka, Japan.
Naoto FujiwaraDepartment of Gastroenterological Surgery, Saitama Medical University International Medical Center, Hidaka, Japan.
Hirofumi SugitaDepartment of Gastroenterological Surgery, Saitama Medical University International Medical Center, Hidaka, Japan.
Hiroshi SatoDepartment of Gastroenterological Surgery, Saitama Medical University International Medical Center, Hidaka, Japan.
Masanori YasudaDepartment of Pathology, Saitama Medical University International Medical Center, Hidaka, Japan.
Shinichi SakuramotoDepartment of Gastroenterological Surgery, Saitama Medical University International Medical Center, Hidaka, Japan.
Shigeki YamaguchiDepartment of Gastroenterological Surgery, Saitama Medical University International Medical Center, Hidaka, Japan.
Saitama Medical University · JP

Funding

No grant is acknowledged in the PubMed record.

6 · The paper itself

Abstract

Alport-leiomyomatosis syndrome is an extremely rare condition occurring at a young age in which Alport syndrome coexists with diffuse leiomyomatosis of the digestive tract (primarily the esophagus). Most patients with diffuse esophageal leiomyomatosis require esophagectomy of variable extents. A 20-year-old man with Alport-leiomyomatosis syndrome was diagnosed with dysphasia and hematuria in childhood. Although he underwent partial esophagogastrectomy at 8 years of age, extremely severe gastroesophageal reflux symptoms were noted postoperatively. He was diagnosed with refractory severe reflux esophagitis associated with diffuse leiomyomatosis and esophagogastric anastomosis, for which he underwent subtotal esophagectomy, gastric tube reconstruction, and esophagogastric anastomosis in the left neck. The postoperative course was generally good, and he had no postoperative reflux symptoms. To achieve long-term control of symptoms, the lesion must be removed completely; nevertheless, unnecessarily extensive esophagectomy should be avoided.

Indexed as

EsophagectomyGastrectomyEsophageal NeoplasmsGastroesophageal RefluxHumansLeiomyomatosisMaleNephritis, HereditaryTomography, X-Ray ComputedYoung AdultAlport–leiomyomatosis syndromeAlport syndromeDiffuse esophageal leiomyomatosisEsophagectomyGastroesophageal reflux disease

Identifiers

PMID31758390
OpenAlexW2991220571

What OpenQuestion holds

Textmetadata
Read underepoch 390

Registered trials

None linked

Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the OpenQuestion graph.