Evidence map›Paper›PMID 31619586›Full record

ArticleJCI insight2019

Brain pharmacology of intrathecal antisense oligonucleotides revealed through multimodal imaging.

Curt Mazur, Berit Powers, Kenneth Zasadny, Jenna M Sullivan, Hemi Dimant, Fredrik Kamme, Jacob Hesterman, John Matson, Michael Oestergaard, Marc Seaman and 14 more

Open access · goldAbstract read
In one paragraph

Article in JCI insight, 2019. The graph could read no effect estimate from its abstract, so it casts no vote on the map. Cited by 71 papers.

0numbers the graph read from it
0cells of the map it votes in
71citing papers in PubMed
6.1field-weighted citation impact, top 3% of its field
1 · What the graph read from it

What it found

Each row is one number read from the abstract, on the scale the paper reported it, with its interval. Left of the dashed line favours the treatment, right favours the comparator. Under each row is the sentence it came from. New to these charts? A ten-minute tutorial.

The abstract states no effect estimate the extractor could read, or names no intervention and outcome on the map, so this paper lights no cell and moves no belief. It is still indexed, cited and linked below.

2 · The registry

The trial behind it

Trials whose registry record cites this paper, or whose number appears in the abstract. A trial that started after this paper was published is citing it as background, not reporting it.

Neither the registry nor the abstract names a trial number. If this is a trial report, that itself is worth knowing.

3 · Its place in the literature

Who cites it

71 citing papers in PubMed, 101 citations in OpenAlex.

  1. Trial
  2. Article
  3. Review
  4. Article
  5. Review
  6. The Versatile Applications of Antisense Oligonucleotides in Modern Medicine.International journal of molecular sciences · 2026
    Review
  7. Observational
  8. Review
  9. Article
  10. Review
  11. Review
  12. Article
  13. Article
  14. Review
  15. Central Nervous System Biodistribution and Pharmacokinetics of Radiolabeled Tofersen in Rodents, Nonhuman Primates, and Humans.Journal of nuclear medicine : official publication, Society of Nuclear Medicine · 2026
    Article
  16. Genetic therapies for neurological diseases.Pharmacological reviews · 2026
    Review
  17. Comparison ofMolecular therapy. Nucleic acids · 2025
    Article
  18. AAV delivery of artificial miRNA targeting MAPT for the reduction of tau pathology in Alzheimer's disease.Molecular therapy : the journal of the American Society of Gene Therapy · 2025
    Article
  19. Article
  20. Article

11 more citing papers are in PubMed but not listed here.

4 · The record

Corrections and comments

PubMed lists nothing against this paper. Absence here is not a guarantee, only a check that was made.

5 · Who and what money

Authors and funding

24 authors at 5 institutions in 2 countries.

Curt MazurIonis Pharmaceuticals, Inc., Carlsbad, California, USA.
Berit PowersIonis Pharmaceuticals, Inc., Carlsbad, California, USA.
Kenneth ZasadnyInvicro, LLC, Boston, Massachusetts, USA.
Jenna M SullivanInvicro, LLC, Boston, Massachusetts, USA.
Hemi DimantInvicro, LLC, Boston, Massachusetts, USA.
Fredrik KammeIonis Pharmaceuticals, Inc., Carlsbad, California, USA.
Jacob HestermanInvicro, LLC, Boston, Massachusetts, USA.
John MatsonIonis Pharmaceuticals, Inc., Carlsbad, California, USA.
Michael OestergaardIonis Pharmaceuticals, Inc., Carlsbad, California, USA.
Marc SeamanInvicro, LLC, Boston, Massachusetts, USA.
Robert W HoltInvicro, LLC, Boston, Massachusetts, USA.
Mohammed QutaishInvicro, LLC, Boston, Massachusetts, USA.
Ildiko PolyakInvicro, LLC, Boston, Massachusetts, USA.
Richard CoelhoInvicro, LLC, Boston, Massachusetts, USA.
Vijay GottumukkalaInvicro, LLC, Boston, Massachusetts, USA.
Carolynn M GautInvicro, LLC, Boston, Massachusetts, USA.
Marc Berridge3D Imaging, Little Rock, Arkansas, USA.
Nazira J AlbargothyUniversity of Southampton, Hampshire, United Kingdom.
Louise KellyUniversity of Southampton, Hampshire, United Kingdom.
Roxana O CarareUniversity of Southampton, Hampshire, United Kingdom.
Jack HoppinInvicro, LLC, Boston, Massachusetts, USA.
Holly KordasiewiczIonis Pharmaceuticals, Inc., Carlsbad, California, USA.
Eric E SwayzeIonis Pharmaceuticals, Inc., Carlsbad, California, USA.
Ajay VermaBiogen, Cambridge, Masschusetts, USA.
Invicro (United States) · USIonis Pharmaceuticals (United States) · USUniversity of Southampton · GBBiogen (United States) · USUniversity of Arkansas at Little Rock · US

Funding

No grant is acknowledged in the PubMed record.

6 · The paper itself

Abstract

Intrathecal (IT) delivery and pharmacology of antisense oligonucleotides (ASOs) for the CNS have been successfully developed to treat spinal muscular atrophy. However, ASO pharmacokinetic (PK) and pharmacodynamic (PD) properties remain poorly understood in the IT compartment. We applied multimodal imaging techniques to elucidate the IT PK and PD of unlabeled, radioactively labeled, or fluorescently labeled ASOs targeting ubiquitously expressed or neuron-specific RNAs. Following lumbar IT bolus injection in rats, all ASOs spread rostrally along the neuraxis, adhered to meninges, and were partially cleared to peripheral lymph nodes and kidneys. Rapid association with the pia and arterial walls preceded passage of ASOs across the glia limitans, along arterial intramural basement membranes, and along white-matter axonal bundles. Several neuronal and glial cell types accumulated ASOs over time, with evidence of probable glial accumulation preceding neuronal uptake. IT doses of anti-GluR1 and anti-Gabra1 ASOs markedly reduced the mRNA and protein levels of their respective neurotransmitter receptor protein targets by 2 weeks and anti-Gabra1 ASOs also reduced binding of the GABAA receptor PET ligand 18F-flumazenil in the brain over 4 weeks. Our multimodal imaging approaches elucidate multiple transport routes underlying the CNS distribution, clearance, and efficacy of IT-dosed ASOs.

Indexed as

AnimalsArteriesBrainFlumazenilGABA-A Receptor AntagonistsGene Knockdown TechniquesHumansInjections, SpinalIntravital MicroscopyMaleMolecular Targeted TherapyMuscular Atrophy, SpinalNeurogliaNeuronsOligonucleotides, AntisensePia Mater2'-fluoroflumazenilFlumazenilGABA-A Receptor AntagonistsGabra1 protein, ratOligonucleotides, AntisenseReceptors, AMPAReceptors, GABA-ARNA, MessengerThionucleotidesNeuroimagingNeurosciencePharmacology

Identifiers

PMID31619586
PMCPMC6824309
OpenAlexW2980602575

What OpenQuestion holds

Textmetadata
Read underepoch 390

Registered trials

None linked

Read under generation 80e0d062 · epoch 390. Bibliography from PubMed, PubMed Central and OpenAlex; grants from NIH RePORTER; trial links from ClinicalTrials.gov; estimates, votes and beliefs from the OpenQuestion graph.